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Loeys-Dietz syndrome

ORPHA:60030Malformation syndromeAutosomal dominant, Autosomal recessiveAntenatal, Infancy, Neonatal

Ассоциированные гены (7)

TGFB2
transforming growth factor beta 2
Disease-causing germline mutation(s) in
OMIM: 190220
TGFB3
transforming growth factor beta 3
Disease-causing germline mutation(s) in
OMIM: 190230
SMAD2
SMAD family member 2
Disease-causing germline mutation(s) in
OMIM: 601366
SMAD3
SMAD family member 3
Disease-causing germline mutation(s) in
OMIM: 603109
IPO8
importin 8
Disease-causing germline mutation(s) (loss of function) in
OMIM: 605600
TGFBR1
transforming growth factor beta receptor 1
Disease-causing germline mutation(s) in
OMIM: 190181
TGFBR2
transforming growth factor beta receptor 2
Disease-causing germline mutation(s) in
OMIM: 190182

Фенотипы (38)

Очень частый (80–99%)8
HP:0001643Patent ductus arteriosus
HP:0001763Pes planus
HP:0002617Dilatation
HP:0002647Aortic dissection
HP:0004942Aortic aneurysm
HP:0005116Arterial tortuosity
HP:0005294Arterial dissection
HP:0100718Uterine rupture
Частый (30–79%)18
HP:0000098Tall stature
HP:0000175Cleft palate
HP:0000193Bifid uvula
HP:0000202Orofacial cleft
HP:0000272Malar flattening
HP:0000316Hypertelorism
HP:0000347Micrognathia
HP:0000592Blue sclerae
HP:0000964Eczematoid dermatitis
HP:0000987Atypical scarring of skin
HP:0001065Striae distensae
HP:0001166Arachnodactyly
HP:0001363Craniosynostosis
HP:0001382Joint hypermobility
HP:0001762Talipes equinovarus
HP:0002099Asthma
HP:0002650Scoliosis
HP:0100490Camptodactyly of finger
Периодический (5–29%)12
HP:0001382Joint hypermobility
HP:0000545Myopia
HP:0000767Pectus excavatum
HP:0000768Pectus carinatum
HP:0000963Thin skin
HP:0000978Bruising susceptibility
HP:0001373Joint dislocation
HP:0001653Mitral regurgitation
HP:0001695Cardiac arrest
HP:0001892Abnormal bleeding
HP:0002108Spontaneous pneumothorax
HP:0410151Eosinophilic infiltration of the esophagus

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы