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Mitochondrial DNA-related progressive external ophthalmoplegia

ORPHA:663DiseaseMitochondrial inheritance, Not applicableAdolescent, Adult

Ассоциированные гены (4)

MT-TS1
mitochondrially encoded tRNA-Ser (UCN) 1
Disease-causing germline mutation(s) in
OMIM: 590080
MT-TL2
mitochondrially encoded tRNA-Leu (CUN) 2
Disease-causing germline mutation(s) in
OMIM: 590055
MT-TN
mitochondrially encoded tRNA-Asn (AAU/C)
Disease-causing germline mutation(s) in
OMIM: 590010
MT-TL1
mitochondrially encoded tRNA-Leu (UUA/G) 1
Candidate gene tested in
OMIM: 590050

Фенотипы (17)

Очень частый (80–99%)2
HP:0000590Progressive external ophthalmoplegia
HP:0003800Muscle abnormality related to mitochondrial dysfunction
Частый (30–79%)12
HP:0000508Ptosis
HP:0000821Hypothyroidism
HP:0001348Brisk reflexes
HP:0002091Restrictive ventilatory defect
HP:0002151Increased circulating lactate concentration
HP:0002747Respiratory insufficiency due to muscle weakness
HP:0003200Ragged-red muscle fibers
HP:0003327Axial muscle weakness
HP:0003457EMG abnormality
HP:0008180Mildly elevated creatine kinase
HP:0008316Abnormal mitochondria in muscle tissue
HP:0009073Progressive proximal muscle weakness
Периодический (5–29%)2
HP:0000716Depression
HP:0001256Intellectual disability, mild
Исключён (0%)1
HP:0000651Diplopia

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы