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Chylomicron retention disease

ORPHA:71DiseaseAutosomal recessiveChildhood, Infancy

Ассоциированные гены (1)

SAR1B
secretion associated Ras related GTPase 1B
Disease-causing germline mutation(s) in
OMIM: 607690

Фенотипы (20)

Облигатный (100%)2
HP:0002014Diarrhea
HP:0003146Hypocholesterolemia
Очень частый (80–99%)4
HP:0000488Retinopathy
HP:0002570Steatorrhea
HP:0002630Fat malabsorption
HP:0002910Elevated circulating hepatic transaminase concentration
Частый (30–79%)6
HP:0001508Failure to thrive
HP:0001510Growth delay
HP:0002013Vomiting
HP:0003270Abdominal distention
HP:0006565Increased hepatocellular lipid droplets
HP:0100508Abnormality of vitamin metabolism
Периодический (5–29%)3
HP:0000505Visual impairment
HP:0001397Hepatic steatosis
HP:0003458EMG: myopathic abnormalities
Очень редкий (1–4%)4
HP:0001284Areflexia
HP:0001927Acanthocytosis
HP:0003198Myopathy
HP:0010831Impaired proprioception
Исключён (0%)1
HP:0002155Hypertriglyceridemia

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы