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Glycogen storage disease due to muscle phosphorylase kinase deficiency

ORPHA:715DiseaseAutosomal recessive, X-linked recessiveAdolescent, Adult

Ассоциированные гены (2)

PHKA1
phosphorylase kinase regulatory subunit alpha 1
Disease-causing germline mutation(s) in
OMIM: 311870
PHKG1
phosphorylase kinase catalytic subunit gamma 1
Candidate gene tested in
OMIM: 172470

Фенотипы (16)

Очень частый (80–99%)1
HP:0003323Progressive muscle weakness
Частый (30–79%)7
HP:0003236Elevated circulating creatine kinase concentration
HP:0003326Myalgia
HP:0003458EMG: myopathic abnormalities
HP:0003546Exercise intolerance
HP:0009051Increased muscle glycogen content
HP:0012378Fatigue
HP:6000198Reduced muscle phosphorylase kinase activity
Периодический (5–29%)8
HP:0100595Camptocormia
HP:0001265Hyporeflexia
HP:0001288Gait disturbance
HP:0002913Myoglobinuria
HP:0003202Skeletal muscle atrophy
HP:0003391Gowers sign
HP:0003394Muscle spasm
HP:0003551Difficulty climbing stairs

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы