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Hereditary hemorrhagic telangiectasia

ORPHA:774DiseaseAutosomal dominantAll ages

Ассоциированные гены (4)

ACVRL1
activin A receptor like type 1
Disease-causing germline mutation(s) in
OMIM: 601284
SMAD4
SMAD family member 4
Disease-causing germline mutation(s) in
OMIM: 600993
ENG
endoglin
Disease-causing germline mutation(s) in
OMIM: 131195
GDF2
growth differentiation factor 2
Disease-causing germline mutation(s) in
OMIM: 605120

Фенотипы (36)

Очень частый (80–99%)8
HP:0000214Lip telangiectasia
HP:0000227Tongue telangiectasia
HP:0000421Epistaxis
HP:0000434Nasal mucosa telangiectasia
HP:0001009Telangiectasia
HP:0004406Spontaneous, recurrent epistaxis
HP:0100579Mucosal telangiectasiae
HP:0100585Telangiectasia of the skin
Частый (30–79%)8
HP:0001409Portal hypertension
HP:0001903Anemia
HP:0002076Migraine
HP:0006548Pulmonary arteriovenous malformation
HP:0006574Hepatic arteriovenous malformation
HP:0011025Abnormality of cardiovascular system physiology
HP:0100026Arteriovenous malformation
HP:0100761Visceral angiomatosis
Периодический (5–29%)20
HP:0000524Conjunctival telangiectasia
HP:0001250Seizure
HP:0001342Cerebral hemorrhage
HP:0001394Cirrhosis
HP:0001399Hepatic failure
HP:0001635Congestive heart failure
HP:0002040Esophageal varix
HP:0002092Pulmonary arterial hypertension
HP:0002105Hemoptysis
HP:0002138Subarachnoid hemorrhage
HP:0002204Pulmonary embolism
HP:0002239Gastrointestinal hemorrhage
HP:0002326Transient ischemic attack
HP:0002408Cerebral arteriovenous malformation
HP:0002629Gastrointestinal arteriovenous malformation
HP:0004936Venous thrombosis
HP:0007763Retinal telangiectasia
HP:0100659Abnormality of the cerebral vasculature
HP:0100784Peripheral arteriovenous fistula
HP:0200008Intestinal polyposis

Эпидемиология (7)

Point prevalence
1-5 / 10 000
Europe
Point prevalence
1-5 / 10 000
France
Point prevalence
1-9 / 100 000
United Kingdom
Point prevalence
1-5 / 10 000
Denmark
Point prevalence
1-5 / 10 000
Japan
Point prevalence
1-9 / 100 000
United States
Point prevalence
1-5 / 10 000
Specific population

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы