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Congenital bile acid synthesis defect type 4

ORPHA:79095DiseaseAutosomal recessiveAll ages

Ассоциированные гены (1)

AMACR
alpha-methylacyl-CoA racemase
Disease-causing germline mutation(s) in
OMIM: 604489

Фенотипы (27)

Очень частый (80–99%)1
HP:0012379Abnormal enzyme/coenzyme activity
Частый (30–79%)5
HP:0000580Pigmentary retinopathy
HP:0001250Seizure
HP:0001298Encephalopathy
HP:0001328Specific learning disability
HP:0007141Sensorimotor neuropathy
Периодический (5–29%)21
HP:0003236Elevated circulating creatine kinase concentration
HP:0005978Type II diabetes mellitus
HP:0011892Low levels of vitamin K
HP:0030516Homonymous hemianopia
HP:0100753Schizophrenia
HP:0200084Giant cell hepatitis
HP:0000135Hypogonadism
HP:0000518Cataract
HP:0000716Depression
HP:0000763Sensory neuropathy
HP:0001081Cholelithiasis
HP:0001251Ataxia
HP:0001268Mental deterioration
HP:0001337Tremor
HP:0002076Migraine
HP:0002354Memory impairment
HP:0002401Stroke-like episode
HP:0002573Hematochezia
HP:0002611Cholestatic liver disease
HP:0002910Elevated circulating hepatic transaminase concentration
HP:0003201Rhabdomyolysis

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы