← Назад

Hydroxykynureninuria

ORPHA:79155DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

KYNU
kynureninase
Disease-causing germline mutation(s) (loss of function) in
OMIM: 605197

Фенотипы (17)

Облигатный (100%)2
HP:0001298Encephalopathy
HP:0004365Abnormality of tryptophan metabolism
Частый (30–79%)13
HP:0000733Abnormal repetitive mannerisms
HP:0000958Dry skin
HP:0001249Intellectual disability
HP:0001263Global developmental delay
HP:0001276Hypertonia
HP:0001649Tachycardia
HP:0001942Metabolic acidosis
HP:0001947Renal tubular acidosis
HP:0002315Headache
HP:0002615Hypotension
HP:0005957Breathing dysregulation
HP:0008527Congenital sensorineural hearing impairment
HP:0010280Stomatitis
Периодический (5–29%)1
HP:0001259Coma
Исключён (0%)1
HP:0002448Progressive encephalopathy

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы