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Isobutyryl-CoA dehydrogenase deficiency

ORPHA:79159DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

ACAD8
acyl-CoA dehydrogenase family member 8
Disease-causing germline mutation(s) (loss of function) in
OMIM: 604773

Фенотипы (11)

Частый (30–79%)3
HP:0003215Dicarboxylic aciduria
HP:0003234Decreased circulating carnitine concentration
HP:0045045Elevated plasma acylcarnitine levels
Периодический (5–29%)8
HP:0000750Delayed speech and language development
HP:0001252Hypotonia
HP:0001642Pulmonic stenosis
HP:0001644Dilated cardiomyopathy
HP:0001944Dehydration
HP:0002013Vomiting
HP:0011342Mild global developmental delay
HP:0012734Ketotic hypoglycemia

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы