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Biotinidase deficiency

ORPHA:79241DiseaseAutosomal recessiveAdolescent, Adult, Childhood, Infancy, Neonatal

Ассоциированные гены (1)

BTD
biotinidase
Disease-causing germline mutation(s) in
OMIM: 609019

Фенотипы (38)

Очень частый (80–99%)3
HP:0001992Organic aciduria
HP:0005979Metabolic ketoacidosis
HP:0410145Decreased biotinidase activity
Частый (30–79%)8
HP:0000407Sensorineural hearing impairment
HP:0000707Abnormality of the nervous system
HP:0000988Skin rash
HP:0001250Seizure
HP:0001252Hypotonia
HP:0001987Hyperammonemia
HP:0002715Abnormality of the immune system
HP:0410263Brain imaging abnormality
Периодический (5–29%)27
HP:0000964Eczematoid dermatitis
HP:0000365Hearing impairment
HP:0000478Abnormality of the eye
HP:0000509Conjunctivitis
HP:0000575Scotoma
HP:0000648Optic atrophy
HP:0001138Optic neuropathy
HP:0001249Intellectual disability
HP:0001251Ataxia
HP:0001254Lethargy
HP:0001263Global developmental delay
HP:0001596Alopecia
HP:0002069Bilateral tonic-clonic seizure
HP:0002098Respiratory distress
HP:0002104Apnea
HP:0002123Generalized myoclonic seizure
HP:0002196Myelopathy
HP:0002313Spastic paraparesis
HP:0002841Recurrent fungal infections
HP:0002883Hyperventilation
HP:0003690Limb muscle weakness
HP:0004429Recurrent viral infections
HP:0005401Recurrent candida infections
HP:0006511Laryngeal stridor
HP:0011153Focal motor seizure
HP:0012469Infantile spasms
HP:0200068Nonprogressive visual loss

Эпидемиология (13)

Prevalence at birth
1-9 / 100 000
Worldwide
Point prevalence
1-9 / 100 000
Worldwide
Prevalence at birth
1-9 / 100 000
United States
Prevalence at birth
1-9 / 100 000
Brazil
Point prevalence
1-9 / 100 000
Europe
Prevalence at birth
1-9 / 100 000
Sweden
Prevalence at birth
1-9 / 100 000
Italy
Point prevalence
1-9 / 100 000
Italy
Prevalence at birth
1-9 / 100 000
Austria
Prevalence at birth
1-9 / 100 000
Hungary
Prevalence at birth
1-9 / 100 000
Turkey
Point prevalence
<1 / 1 000 000
China
Prevalence at birth
1-5 / 10 000
Czech Republic

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы