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Pyruvate dehydrogenase phosphatase deficiency

ORPHA:79246Clinical subtypeAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

PDP1
pyruvate dehydrogenase phosphatase catalytic subunit 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 605993

Фенотипы (11)

Очень частый (80–99%)1
HP:0002928Decreased activity of the pyruvate dehydrogenase complex
Частый (30–79%)10
HP:0001319Neonatal hypotonia
HP:0002151Increased circulating lactate concentration
HP:0003128Lactic acidosis
HP:0003348Hyperalaninemia
HP:0003648Lacticaciduria
HP:0008358Hyperprolinemia
HP:0008936Axial hypotonia
HP:0011342Mild global developmental delay
HP:0040328Focal hyperintensity of cerebral white matter on MRI
HP:0410263Brain imaging abnormality

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы