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Congenital bile acid synthesis defect type 1

ORPHA:79301DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

HSD3B7
hydroxy-delta-5-steroid dehydrogenase, 3 beta- and steroid delta-isomerase 7
Disease-causing germline mutation(s) in
OMIM: 607764

Фенотипы (16)

Очень частый (80–99%)7
HP:0000952Jaundice
HP:0001080Biliary tract abnormality
HP:0001508Failure to thrive
HP:0002024Malabsorption
HP:0002240Hepatomegaly
HP:0002910Elevated circulating hepatic transaminase concentration
HP:0006566Neonatal cholestatic liver disease
Частый (30–79%)3
HP:0001744Splenomegaly
HP:0001928Abnormality of coagulation
HP:0002239Gastrointestinal hemorrhage
Периодический (5–29%)6
HP:0000662Nyctalopia
HP:0000939Osteoporosis
HP:0000989Pruritus
HP:0001394Cirrhosis
HP:0001892Abnormal bleeding
HP:0009830Peripheral neuropathy

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы