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D-2-hydroxyglutaric aciduria

ORPHA:79315DiseaseAutosomal dominant, Autosomal recessiveChildhood, Infancy, Neonatal

Ассоциированные гены (2)

D2HGDH
D-2-hydroxyglutarate dehydrogenase
Disease-causing germline mutation(s) in
OMIM: 609186
IDH2
isocitrate dehydrogenase (NADP(+)) 2
Disease-causing germline mutation(s) (gain of function) in
OMIM: 147650

Фенотипы (13)

Очень частый (80–99%)4
HP:0001263Global developmental delay
HP:0012321D-2-hydroxyglutaric aciduria
HP:0040146D-2-hydroxyglutaric acidemia
HP:6000246Elevated CSF D-2-hydroxyglutaric acid concentration
Частый (30–79%)2
HP:0001250Seizure
HP:0001252Hypotonia
Периодический (5–29%)7
HP:0000750Delayed speech and language development
HP:0001298Encephalopathy
HP:0001638Cardiomyopathy
HP:0002119Ventriculomegaly
HP:0010307Stridor
HP:0012448Delayed myelination
HP:0100704Cerebral visual impairment

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы