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MPI-CDG

ORPHA:79319DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

MPI
mannose phosphate isomerase
Disease-causing germline mutation(s) in
OMIM: 154550

Фенотипы (22)

Облигатный (100%)1
HP:0012379Abnormal enzyme/coenzyme activity
Очень частый (80–99%)6
HP:0001395Hepatic fibrosis
HP:0002014Diarrhea
HP:0002240Hepatomegaly
HP:0003073Hypoalbuminemia
HP:0003256Abnormality of the coagulation cascade
HP:0040246Reduced antithrombin antigen
Частый (30–79%)12
HP:0000825Hyperinsulinemic hypoglycemia
HP:0000969Edema
HP:0001409Portal hypertension
HP:0001410Decreased liver function
HP:0001508Failure to thrive
HP:0001929Reduced factor XI activity
HP:0001977Abnormal thrombosis
HP:0002013Vomiting
HP:0002239Gastrointestinal hemorrhage
HP:0002243Protein-losing enteropathy
HP:0004855Reduced protein S activity
HP:0005543Reduced protein C activity
Периодический (5–29%)1
HP:0000821Hypothyroidism
Исключён (0%)2
HP:0000707Abnormality of the nervous system
HP:0001249Intellectual disability

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы