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MPDU1-CDG

ORPHA:79323DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

MPDU1
mannose-P-dolichol utilization defect 1
Disease-causing germline mutation(s) in
OMIM: 604041

Фенотипы (26)

Очень частый (80–99%)3
HP:0003642Type I transferrin isoform profile
HP:0010864Intellectual disability, severe
HP:0012379Abnormal enzyme/coenzyme activity
Частый (30–79%)1
HP:0008947Floppy infant
Периодический (5–29%)22
HP:0000233Thin vermilion border
HP:0000242Parietal bossing
HP:0000260Wide anterior fontanel
HP:0000648Optic atrophy
HP:0000803Renal cortical cysts
HP:0000824Decreased response to growth hormone stimulation test
HP:0000964Eczematoid dermatitis
HP:0001250Seizure
HP:0001276Hypertonia
HP:0002119Ventriculomegaly
HP:0002521Hypsarrhythmia
HP:0003236Elevated circulating creatine kinase concentration
HP:0005478Prominent frontal sinuses
HP:0007965Undetectable visual evoked potentials
HP:0008064Ichthyosis
HP:0008529Absence of acoustic reflex
HP:0011968Feeding difficulties
HP:0012704Widened subarachnoid space
HP:0025474Erythematous plaque
HP:0030353Decreased serum insulin-like growth factor 1
HP:0040189Scaling skin
HP:0040288Nasogastric tube feeding

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы