← Назад

Spondyloepimetaphyseal dysplasia, Shohat type

ORPHA:93352DiseaseAutosomal recessiveAntenatal, Infancy, Neonatal

Ассоциированные гены (1)

DDRGK1
DDRGK domain containing 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 616177

Фенотипы (33)

Частый (30–79%)14
HP:0000926Platyspondyly
HP:0002650Scoliosis
HP:0002829Arthralgia
HP:0003015Flared metaphysis
HP:0003016Metaphyseal widening
HP:0003026Short long bone
HP:0003088Premature osteoarthritis
HP:0003468Abnormal vertebral morphology
HP:0003498Disproportionate short stature
HP:0003510Severe short stature
HP:0005257Thoracic hypoplasia
HP:0005930Abnormality of epiphysis morphology
HP:0006462Generalized bone demineralization
HP:0008463Central vertebral hypoplasia
Периодический (5–29%)19
HP:0000470Short neck
HP:0001433Hepatosplenomegaly
HP:0001602Laryngeal stenosis
HP:0001609Hoarse voice
HP:0002663Delayed epiphyseal ossification
HP:0002777Tracheal stenosis
HP:0002781Upper airway obstruction
HP:0002953Vertebral compression fracture
HP:0002970Genu varum
HP:0002979Bowing of the legs
HP:0003025Metaphyseal irregularity
HP:0003099Fibular overgrowth
HP:0003270Abdominal distention
HP:0003307Hyperlordosis
HP:0008418Squared-off platyspondyly
HP:0008450Narrow vertebral interpedicular distance
HP:0009826Limb undergrowth
HP:0025426Abnormal bronchus morphology
HP:0001382Joint hypermobility

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы