← Назад

Spinocerebellar ataxia with axonal neuropathy type 1

ORPHA:94124DiseaseAutosomal recessiveAdolescent

Ассоциированные гены (1)

TDP1
tyrosyl-DNA phosphodiesterase 1
Disease-causing germline mutation(s) in
OMIM: 607198

Фенотипы (20)

Частый (30–79%)18
HP:0000640Gaze-evoked nystagmus
HP:0001251Ataxia
HP:0001284Areflexia
HP:0001761Pes cavus
HP:0002166Impaired vibration sensation in the lower limbs
HP:0002283Global brain atrophy
HP:0002464Spastic dysarthria
HP:0002503Spinocerebellar tract degeneration
HP:0003073Hypoalbuminemia
HP:0003124Hypercholesterolemia
HP:0003376Steppage gait
HP:0003693Distal amyotrophy
HP:0006855Cerebellar vermis atrophy
HP:0006858Impaired distal proprioception
HP:0007021Pain insensitivity
HP:0007141Sensorimotor neuropathy
HP:0009053Distal lower limb muscle weakness
HP:0009830Peripheral neuropathy
Периодический (5–29%)1
HP:0001250Seizure
Исключён (0%)1
HP:0001249Intellectual disability

Эпидемиология (2)

Point prevalence
<1 / 1 000 000
Worldwide
Cases/families
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы