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Autosomal recessive spinocerebellar ataxia-blindness-deafness syndrome

ORPHA:95433DiseaseAutosomal recessiveChildhood

Ассоциированные гены (1)

PEX6
peroxisomal biogenesis factor 6
Disease-causing germline mutation(s) in
OMIM: 601498

Фенотипы (19)

Частый (30–79%)18
HP:0001288Gait disturbance
HP:0000365Hearing impairment
HP:0000524Conjunctival telangiectasia
HP:0000618Blindness
HP:0000639Nystagmus
HP:0000648Optic atrophy
HP:0000763Sensory neuropathy
HP:0002066Gait ataxia
HP:0002073Progressive cerebellar ataxia
HP:0002166Impaired vibration sensation in the lower limbs
HP:0002346Head tremor
HP:0002464Spastic dysarthria
HP:0005102Cochlear degeneration
HP:0006254Elevated alpha-fetoprotein
HP:0007126Proximal amyotrophy
HP:0007141Sensorimotor neuropathy
HP:0007263Spinocerebellar atrophy
HP:0008180Mildly elevated creatine kinase
Исключён (0%)1
HP:0000657Oculomotor apraxia

Эпидемиология (2)

Point prevalence
<1 / 1 000 000
Worldwide
Cases/families
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы