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Charcot-Marie-Tooth disease type 2B1

ORPHA:98856DiseaseAutosomal recessiveChildhood

Ассоциированные гены (1)

LMNA
lamin A/C
Disease-causing germline mutation(s) in
OMIM: 150330

Фенотипы (33)

Очень частый (80–99%)9
HP:0002936Distal sensory impairment
HP:0003380Decreased number of peripheral myelinated nerve fibers
HP:0003390Sensory axonal neuropathy
HP:0003447Axonal loss
HP:0003482EMG: axonal abnormality
HP:0007002Motor axonal neuropathy
HP:0007078Decreased amplitude of sensory action potentials
HP:0009053Distal lower limb muscle weakness
HP:0040078Axonal degeneration
Частый (30–79%)17
HP:0001284Areflexia
HP:0001760Abnormal foot morphology
HP:0001761Pes cavus
HP:0001765Hammertoe
HP:0002460Distal muscle weakness
HP:0003376Steppage gait
HP:0003387Decreased number of large peripheral myelinated nerve fibers
HP:0003693Distal amyotrophy
HP:0003701Proximal muscle weakness
HP:0007149Distal upper limb amyotrophy
HP:0008956Proximal lower limb amyotrophy
HP:0008959Distal upper limb muscle weakness
HP:0008994Proximal muscle weakness in lower limbs
HP:0009049Peroneal muscle atrophy
HP:0009130Hand muscle atrophy
HP:0011916Toe extensor amyotrophy
HP:0030237Hand muscle weakness
Периодический (5–29%)5
HP:0002540Inability to walk
HP:0003724Shoulder girdle muscle atrophy
HP:0007126Proximal amyotrophy
HP:0007249Decreased number of small peripheral myelinated nerve fibers
HP:0008988Pelvic girdle muscle atrophy
Очень редкий (1–4%)1
HP:0003431Decreased motor nerve conduction velocity
Исключён (0%)1
HP:0007233Clusters of axonal regeneration

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы