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Autosomal dominant spastic paraplegia type 10

ORPHA:100991DiseaseAutosomal dominantAdolescent, Adult, Childhood

Ассоциированные гены (1)

KIF5A
kinesin family member 5A
Disease-causing germline mutation(s) in
OMIM: 602821

Фенотипы (28)

Облигатный (100%)1
HP:0002061Lower limb spasticity
Очень частый (80–99%)2
HP:0002395Lower limb hyperreflexia
HP:0008944Distal lower limb amyotrophy
Частый (30–79%)12
HP:0003487Babinski sign
HP:0000510Rod-cone dystrophy
HP:0002936Distal sensory impairment
HP:0003477Peripheral axonal neuropathy
HP:0031958Spastic paraparetic gait
HP:0002493Upper motor neuron dysfunction
HP:0006886Impaired distal vibration sensation
HP:0007350Hyperreflexia in upper limbs
HP:0000012Urinary urgency
HP:0008969Leg muscle stiffness
HP:0007340Lower limb muscle weakness
HP:0005340Spastic/hyperactive bladder
Периодический (5–29%)7
HP:0001761Pes cavus
HP:0007141Sensorimotor neuropathy
HP:0009129Upper limb amyotrophy
HP:0002342Intellectual disability, moderate
HP:0003401Paresthesia
HP:0002619Varicose veins
HP:0005679Dupuytren contracture
Очень редкий (1–4%)6
HP:0001300Parkinsonism
HP:0000365Hearing impairment
HP:0100543Cognitive impairment
HP:0011448Ankle clonus
HP:0006986Upper limb spasticity
HP:0002650Scoliosis

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы