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Distal hereditary motor neuropathy type 5

ORPHA:139536DiseaseAutosomal dominantAdolescent, Adult, Childhood

Ассоциированные гены (3)

REEP1
receptor accessory protein 1
Disease-causing germline mutation(s) in
OMIM: 609139
BSCL2
BSCL2 lipid droplet biogenesis associated, seipin
Disease-causing germline mutation(s) in
OMIM: 606158
GARS1
glycyl-tRNA synthetase 1
Disease-causing germline mutation(s) in
OMIM: 600287

Фенотипы (16)

Частый (30–79%)11
HP:0002317Unsteady gait
HP:0002495Impaired vibratory sensation
HP:0003392First dorsal interossei muscle weakness
HP:0003393Thenar muscle atrophy
HP:0003426First dorsal interossei muscle atrophy
HP:0003427Thenar muscle weakness
HP:0003435Cold-induced hand cramps
HP:0003484Upper limb muscle weakness
HP:0003693Distal amyotrophy
HP:0007178Motor polyneuropathy
HP:0009053Distal lower limb muscle weakness
Периодический (5–29%)4
HP:0001347Hyperreflexia
HP:0001761Pes cavus
HP:0001765Hammertoe
HP:0008081Pes valgus
Очень редкий (1–4%)1
HP:0040131Abnormal motor nerve conduction velocity

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы