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Xq21 microdeletion syndrome

ORPHA:1435Malformation syndromeX-linked recessiveInfancy, Neonatal

Ассоциированные гены (1)

POU3F4
POU class 3 homeobox 4
Disease-causing germline mutation(s) in
OMIM: 300039

Фенотипы (39)

Очень частый (80–99%)4
HP:0000407Sensorineural hearing impairment
HP:0000532Chorioretinal abnormality
HP:0001139Choroideremia
HP:0200065Chorioretinal degeneration
Частый (30–79%)25
HP:0000375Abnormal cochlea morphology
HP:0000381Stapes ankylosis
HP:0000405Conductive hearing impairment
HP:0000648Optic atrophy
HP:0000824Decreased response to growth hormone stimulation test
HP:0000830Anterior hypopituitarism
HP:0001251Ataxia
HP:0001256Intellectual disability, mild
HP:0001263Global developmental delay
HP:0001347Hyperreflexia
HP:0001510Growth delay
HP:0001513Obesity
HP:0002066Gait ataxia
HP:0002750Delayed skeletal maturation
HP:0004458Dilatated internal auditory canal
HP:0005109Abnormality of the Achilles tendon
HP:0007663Reduced visual acuity
HP:0007675Progressive night blindness
HP:0007937Reticular pigmentary degeneration
HP:0007994Peripheral visual field loss
HP:0008245Pituitary hypothyroidism
HP:0008619Bilateral sensorineural hearing impairment
HP:0008897Postnatal growth retardation
HP:0011448Ankle clonus
HP:0030532Visual acuity test abnormality
Периодический (5–29%)7
HP:0000486Strabismus
HP:0000639Nystagmus
HP:0000822Hypertension
HP:0001250Seizure
HP:0001920Renal artery stenosis
HP:0002075Dysdiadochokinesis
HP:0003484Upper limb muscle weakness
Исключён (0%)3
HP:0000863Central diabetes insipidus
HP:0010625Anterior pituitary dysgenesis
HP:0011748Adrenocorticotropic hormone deficiency

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы