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Primary sclerosing cholangitis

ORPHA:171DiseaseMultigenic/multifactorialAdolescent, Adult, Childhood, Elderly

Ассоциированные гены (4)

SEMA4D
semaphorin 4D
Disease-causing germline mutation(s) in
OMIM: 601866
GPR35
G protein-coupled receptor 35
Major susceptibility factor in
OMIM: 602646
MST1
macrophage stimulating 1
Major susceptibility factor in
OMIM: 142408
TCF4
transcription factor 4
Major susceptibility factor in
OMIM: 602272

Фенотипы (55)

Очень частый (80–99%)3
HP:0001396Cholestasis
HP:0002960Autoimmunity
HP:0012440Abnormal biliary tract morphology
Частый (30–79%)16
HP:0001394Cirrhosis
HP:0001395Hepatic fibrosis
HP:0001409Portal hypertension
HP:0001433Hepatosplenomegaly
HP:0001541Ascites
HP:0001744Splenomegaly
HP:0001824Weight loss
HP:0001945Fever
HP:0002240Hepatomegaly
HP:0002910Elevated circulating hepatic transaminase concentration
HP:0010638Elevated alkaline phosphatase of hepatic origin
HP:0012522Spider hemangioma
HP:0012700Abnormal large intestine physiology
HP:0030168Dilated superficial abdominal veins
HP:0100279Ulcerative colitis
HP:0100869Palmar telangiectasia
Периодический (5–29%)28
HP:0000083Renal insufficiency
HP:0000716Depression
HP:0000938Osteopenia
HP:0000939Osteoporosis
HP:0000952Jaundice
HP:0000989Pruritus
HP:0001081Cholelithiasis
HP:0001402Hepatocellular carcinoma
HP:0001635Congestive heart failure
HP:0001733Pancreatitis
HP:0002027Abdominal pain
HP:0002202Pleural effusion
HP:0002608Celiac disease
HP:0003073Hypoalbuminemia
HP:0003459Polyclonal elevation of IgM
HP:0003700Generalized amyotrophy
HP:0004905Low levels of vitamin A
HP:0008151Prolonged prothrombin time
HP:0011892Low levels of vitamin K
HP:0012115Hepatitis
HP:0012378Fatigue
HP:0030153Cholangiocarcinoma
HP:0040275Adenocarcinoma of the large intestine
HP:0100512Low levels of vitamin D
HP:0100513Low levels of vitamin E
HP:0100626Chronic hepatic failure
HP:0100646Thyroiditis
HP:0100651Type I diabetes mellitus
Очень редкий (1–4%)4
HP:0000554Uveitis
HP:0001298Encephalopathy
HP:0006554Acute hepatic failure
HP:0100575Neoplasm of the gallbladder
Исключён (0%)4
HP:0001879Abnormality of eosinophils
HP:0005429Recurrent systemic pyogenic infections
HP:0011034Amyloidosis
HP:0100727Histiocytosis

Эпидемиология (18)

Annual incidence
1-9 / 1 000 000
Europe
Point prevalence
1-9 / 100 000
Europe
Point prevalence
1-9 / 100 000
Worldwide
Annual incidence
1-9 / 1 000 000
Worldwide
Annual incidence
1-9 / 1 000 000
United States
Point prevalence
1-9 / 100 000
United States
Annual incidence
1-9 / 100 000
Norway
Point prevalence
1-9 / 100 000
Norway
Annual incidence
1-9 / 100 000
Sweden
Point prevalence
1-5 / 10 000
Sweden
Annual incidence
1-9 / 1 000 000
United Kingdom
Point prevalence
1-9 / 100 000
United Kingdom
Annual incidence
1-9 / 1 000 000
Netherlands
Point prevalence
1-9 / 100 000
Netherlands
Annual incidence
1-9 / 1 000 000
Canada
Annual incidence
<1 / 1 000 000
Spain
Point prevalence
1-9 / 1 000 000
Spain
Point prevalence
1-9 / 100 000
Singapore

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы