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Typical nemaline myopathy

ORPHA:171436DiseaseAutosomal dominant, Autosomal recessiveAntenatal, Neonatal

Ассоциированные гены (6)

ACTA1
actin alpha 1, skeletal muscle
Disease-causing germline mutation(s) in
OMIM: 102610
CFL2
cofilin 2
Disease-causing germline mutation(s) in
OMIM: 601443
TPM2
tropomyosin 2
Disease-causing germline mutation(s) in
OMIM: 190990
NEB
nebulin
Disease-causing germline mutation(s) in
OMIM: 161650
KLHL41
kelch like family member 41
Disease-causing germline mutation(s) (loss of function) in
OMIM: 607701
LMOD3
leiomodin 3
Disease-causing germline mutation(s) (loss of function) in
OMIM: 616112

Фенотипы (39)

Частый (30–79%)13
HP:0000218High palate
HP:0001265Hyporeflexia
HP:0001288Gait disturbance
HP:0001319Neonatal hypotonia
HP:0002093Respiratory insufficiency
HP:0003325Limb-girdle muscle weakness
HP:0003327Axial muscle weakness
HP:0003557Increased variability in muscle fiber diameter
HP:0003722Neck flexor weakness
HP:0003803Type 1 muscle fiber predominance
HP:0009027Foot dorsiflexor weakness
HP:0010628Facial palsy
HP:0030198Fatigable weakness of distal limb muscles
Периодический (5–29%)25
HP:0000275Narrow face
HP:0000347Micrognathia
HP:0000470Short neck
HP:0000508Ptosis
HP:0000767Pectus excavatum
HP:0000774Narrow chest
HP:0001349Facial diplegia
HP:0001371Flexion contracture
HP:0001561Polyhydramnios
HP:0002375Hypokinesia
HP:0002515Waddling gait
HP:0002650Scoliosis
HP:0002804Arthrogryposis multiplex congenita
HP:0002827Hip dislocation
HP:0002857Genu valgum
HP:0002877Nocturnal hypoventilation
HP:0002970Genu varum
HP:0003198Myopathy
HP:0003236Elevated circulating creatine kinase concentration
HP:0003306Spinal rigidity
HP:0003307Hyperlordosis
HP:0003798Nemaline bodies
HP:0011968Feeding difficulties
HP:0030196Fatigable weakness of respiratory muscles
HP:0030200Fatiguable weakness of proximal limb muscles
Очень редкий (1–4%)1
HP:0002808Kyphosis

Эпидемиология (1)

Point prevalence
1-9 / 100 000
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы