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EAST syndrome

ORPHA:199343DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

KCNJ10
potassium inwardly rectifying channel subfamily J member 10
Disease-causing germline mutation(s) in
OMIM: 602208

Фенотипы (26)

Очень частый (80–99%)16
HP:0001249Intellectual disability
HP:0001250Seizure
HP:0001251Ataxia
HP:0001263Global developmental delay
HP:0002197Generalized-onset seizure
HP:0002900Hypokalemia
HP:0002917Hypomagnesemia
HP:0005567Renal magnesium wasting
HP:0012591Abnormal urinary electrolyte concentration
HP:0012606Renal sodium wasting
HP:0030083Salt craving
HP:0200114Metabolic alkalosis
HP:0000127Renal salt wasting
HP:0000407Sensorineural hearing impairment
HP:0000848Increased circulating renin level
HP:0000859Hyperaldosteronism
Частый (30–79%)3
HP:0000805Enuresis
HP:0001959Polydipsia
HP:0002345Action tremor
Периодический (5–29%)7
HP:0001272Cerebellar atrophy
HP:0001288Gait disturbance
HP:0001344Absent speech
HP:0002540Inability to walk
HP:0003477Peripheral axonal neuropathy
HP:0007182Peripheral hypomyelination
HP:0007340Lower limb muscle weakness

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы