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Xeroderma pigmentosum-Cockayne syndrome complex

ORPHA:220295DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (4)

ERCC5
ERCC excision repair 5, endonuclease
Disease-causing germline mutation(s) in
OMIM: 133530
ERCC4
ERCC excision repair 4, endonuclease catalytic subunit
Disease-causing germline mutation(s) in
OMIM: 133520
ERCC2
ERCC excision repair 2, TFIIH core complex helicase subunit
Disease-causing germline mutation(s) in
OMIM: 126340
ERCC3
ERCC excision repair 3, TFIIH core complex helicase subunit
Disease-causing germline mutation(s) in
OMIM: 133510

Фенотипы (29)

Очень частый (80–99%)21
HP:0000238Hydrocephalus
HP:0000252Microcephaly
HP:0000365Hearing impairment
HP:0000488Retinopathy
HP:0000639Nystagmus
HP:0000648Optic atrophy
HP:0000958Dry skin
HP:0000988Skin rash
HP:0000992Cutaneous photosensitivity
HP:0001025Urticaria
HP:0001029Poikiloderma
HP:0001249Intellectual disability
HP:0001251Ataxia
HP:0001257Spasticity
HP:0002634Arteriosclerosis
HP:0004322Short stature
HP:0004326Cachexia
HP:0004334Dermal atrophy
HP:0004337Abnormality of amino acid metabolism
HP:0007495Prematurely aged appearance
HP:0007587Numerous pigmented freckles
Частый (30–79%)8
HP:0000651Diplopia
HP:0001260Dysarthria
HP:0001263Global developmental delay
HP:0001289Confusion
HP:0002671Basal cell carcinoma
HP:0002861Melanoma
HP:0006739Squamous cell carcinoma of the skin
HP:0007108Demyelinating peripheral neuropathy

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы