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Joubert syndrome with renal defect

ORPHA:220497Malformation syndromeAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (3)

NPHP1
nephrocystin 1
Disease-causing germline mutation(s) in
OMIM: 607100
RPGRIP1L
RPGRIP1 like
Disease-causing germline mutation(s) in
OMIM: 610937
TMEM237
transmembrane protein 237
Disease-causing germline mutation(s) in
OMIM: 614423

Фенотипы (36)

Очень частый (80–99%)10
HP:0000112Nephropathy
HP:0000657Oculomotor apraxia
HP:0001249Intellectual disability
HP:0001251Ataxia
HP:0001252Hypotonia
HP:0001263Global developmental delay
HP:0001320Cerebellar vermis hypoplasia
HP:0002104Apnea
HP:0002419Molar tooth sign on MRI
HP:0002793Abnormal pattern of respiration
Частый (30–79%)6
HP:0000276Long face
HP:0000358Posteriorly rotated ears
HP:0000639Nystagmus
HP:0001288Gait disturbance
HP:0004422Biparietal narrowing
HP:0011968Feeding difficulties
Периодический (5–29%)20
HP:0000083Renal insufficiency
HP:0000175Cleft palate
HP:0000202Orofacial cleft
HP:0000238Hydrocephalus
HP:0000426Prominent nasal bridge
HP:0000463Anteverted nares
HP:0000486Strabismus
HP:0000508Ptosis
HP:0000612Iris coloboma
HP:0000864Abnormality of the hypothalamus-pituitary axis
HP:0001161Hand polydactyly
HP:0001250Seizure
HP:0001274Agenesis of corpus callosum
HP:0001337Tremor
HP:0002084Encephalocele
HP:0002126Polymicrogyria
HP:0002251Aganglionic megacolon
HP:0002553Highly arched eyebrow
HP:0002650Scoliosis
HP:0030680Abnormal cardiovascular system morphology

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы