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Frontotemporal dementia with motor neuron disease

ORPHA:275872DiseaseAutosomal dominantAdult

Ассоциированные гены (7)

VCP
valosin containing protein
Disease-causing germline mutation(s) in
OMIM: 601023
TARDBP
TAR DNA binding protein
Disease-causing germline mutation(s) in
OMIM: 605078
FUS
FUS RNA binding protein
Major susceptibility factor in
OMIM: 137070
SQSTM1
sequestosome 1
Disease-causing germline mutation(s) in
OMIM: 601530
C9ORF72
C9orf72-SMCR8 complex subunit
Disease-causing germline mutation(s) in
OMIM: 614260
TBK1
TANK binding kinase 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 604834
CHCHD10
coiled-coil-helix-coiled-coil-helix domain containing 10
Disease-causing germline mutation(s) in
OMIM: 615903

Фенотипы (35)

Очень частый (80–99%)3
HP:0002366Abnormal lower motor neuron morphology
HP:0002127Abnormal upper motor neuron morphology
HP:0002145Frontotemporal dementia
Частый (30–79%)20
HP:0000708Atypical behavior
HP:0000716Depression
HP:0000738Hallucinations
HP:0000741Apathy
HP:0001260Dysarthria
HP:0001300Parkinsonism
HP:0002015Dysphagia
HP:0002071Abnormality of extrapyramidal motor function
HP:0002073Progressive cerebellar ataxia
HP:0002171Gliosis
HP:0002186Apraxia
HP:0002273Tetraparesis
HP:0002314Degeneration of the lateral corticospinal tracts
HP:0002385Paraparesis
HP:0002442Dyscalculia
HP:0002460Distal muscle weakness
HP:0003700Generalized amyotrophy
HP:0003701Proximal muscle weakness
HP:0007190Neuronal loss in the cerebral cortex
HP:0010549Weakness due to upper motor neuron dysfunction
Периодический (5–29%)11
HP:0000605Supranuclear gaze palsy
HP:0000734Disinhibition
HP:0001265Hyporeflexia
HP:0001283Bulbar palsy
HP:0002283Global brain atrophy
HP:0002300Mutism
HP:0002380Fasciculations
HP:0003487Babinski sign
HP:0008322Abnormal mitochondrial morphology
HP:0008619Bilateral sensorineural hearing impairment
HP:0030223Perseveration
Очень редкий (1–4%)1
HP:0000508Ptosis

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы