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Juvenile amyotrophic lateral sclerosis

ORPHA:300605DiseaseAutosomal recessiveChildhood

Ассоциированные гены (5)

ALS2
alsin Rho guanine nucleotide exchange factor ALS2
Disease-causing germline mutation(s) in
OMIM: 606352
SPG11
SPG11 vesicle trafficking associated, spatacsin
Disease-causing germline mutation(s) in
OMIM: 610844
SIGMAR1
sigma non-opioid intracellular receptor 1
Disease-causing germline mutation(s) in
OMIM: 601978
FUS
FUS RNA binding protein
Disease-causing germline mutation(s) in
OMIM: 137070
SPTLC1
serine palmitoyltransferase long chain base subunit 1
Disease-causing germline mutation(s) in
OMIM: 605712

Фенотипы (46)

Очень частый (80–99%)6
HP:0001324Muscle weakness
HP:0002061Lower limb spasticity
HP:0003202Skeletal muscle atrophy
HP:0003693Distal amyotrophy
HP:0006986Upper limb spasticity
HP:0007354Amyotrophic lateral sclerosis
Частый (30–79%)15
HP:0001264Spastic diplegia
HP:0001276Hypertonia
HP:0001288Gait disturbance
HP:0001332Dystonia
HP:0001348Brisk reflexes
HP:0002167Abnormality of speech or vocalization
HP:0002460Distal muscle weakness
HP:0002483Bulbar signs
HP:0002540Inability to walk
HP:0003429CNS hypomyelination
HP:0005750Contractures of the joints of the lower limbs
HP:0031936Delayed ability to walk
HP:0031960Arm dystonia
HP:0100295Muscle fiber atrophy
HP:0100360Contractures of the joints of the upper limbs
Периодический (5–29%)25
HP:0000020Urinary incontinence
HP:0000252Microcephaly
HP:0000605Supranuclear gaze palsy
HP:0000639Nystagmus
HP:0000708Atypical behavior
HP:0001251Ataxia
HP:0001263Global developmental delay
HP:0001300Parkinsonism
HP:0001317Abnormal cerebellum morphology
HP:0002015Dysphagia
HP:0002072Chorea
HP:0002169Clonus
HP:0002179Opisthotonus
HP:0002425Anarthria
HP:0002530Axial dystonia
HP:0002544Retrocollis
HP:0002599Head titubation
HP:0002650Scoliosis
HP:0003701Proximal muscle weakness
HP:0003722Neck flexor weakness
HP:0004326Cachexia
HP:0011471Gastrostomy tube feeding in infancy
HP:0012048Oromandibular dystonia
HP:0030051Tip-toe gait
HP:0100543Cognitive impairment

Эпидемиология (1)

Point prevalence
<1 / 1 000 000
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы