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Combined oxidative phosphorylation defect type 13

ORPHA:319514DiseaseAutosomal recessiveInfancy

Ассоциированные гены (1)

PNPT1
polyribonucleotide nucleotidyltransferase 1
Disease-causing germline mutation(s) in
OMIM: 610316

Фенотипы (33)

Очень частый (80–99%)2
HP:0002151Increased circulating lactate concentration
HP:0200125Mitochondrial respiratory chain defects
Частый (30–79%)12
HP:0000407Sensorineural hearing impairment
HP:0000639Nystagmus
HP:0001266Choreoathetosis
HP:0001290Generalized hypotonia
HP:0001324Muscle weakness
HP:0002421Poor head control
HP:0002451Limb dystonia
HP:0002490Increased CSF lactate
HP:0007069Profound static encephalopathy
HP:0008936Axial hypotonia
HP:0010994Abnormal corpus striatum morphology
HP:0012448Delayed myelination
Периодический (5–29%)19
HP:0001511Intrauterine growth retardation
HP:0002134Abnormality of the basal ganglia
HP:0002310Orofacial dyskinesia
HP:0003273Hip contracture
HP:0003548Subsarcolemmal accumulations of abnormally shaped mitochondria
HP:0003554Type 2 muscle fiber atrophy
HP:0003803Type 1 muscle fiber predominance
HP:0006466Ankle flexion contracture
HP:0006895Lower limb hypertonia
HP:0011471Gastrostomy tube feeding in infancy
HP:0011968Feeding difficulties
HP:0040204Elevated CSF neopterin level
HP:0000496Abnormality of eye movement
HP:0000519Developmental cataract
HP:0000762Decreased nerve conduction velocity
HP:0000763Sensory neuropathy
HP:0001273Abnormal corpus callosum morphology
HP:0001344Absent speech
HP:0001508Failure to thrive

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы