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Familial infantile myoclonic epilepsy

ORPHA:352582DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (3)

CPLX1
complexin 1
Disease-causing germline mutation(s) in
OMIM: 605032
TBC1D24
TBC1 domain family member 24
Disease-causing germline mutation(s) (loss of function) in
OMIM: 613577
SCN8A
sodium voltage-gated channel alpha subunit 8
Disease-causing germline mutation(s) in
OMIM: 600702

Фенотипы (25)

Очень частый (80–99%)2
HP:0001250Seizure
HP:0002123Generalized myoclonic seizure
Частый (30–79%)8
HP:0001260Dysarthria
HP:0001272Cerebellar atrophy
HP:0006891Thick cerebral cortex
HP:0007359Focal-onset seizure
HP:0011171Simple febrile seizures
HP:0011197EEG with focal spike waves
HP:0025190Bilateral tonic-clonic seizure with generalized onset
HP:0025373Interictal EEG abnormality
Периодический (5–29%)15
HP:0000520Proptosis
HP:0000643Blepharospasm
HP:0000750Delayed speech and language development
HP:0001251Ataxia
HP:0001256Intellectual disability, mild
HP:0001263Global developmental delay
HP:0001270Motor delay
HP:0001288Gait disturbance
HP:0002069Bilateral tonic-clonic seizure
HP:0002312Clumsiness
HP:0002342Intellectual disability, moderate
HP:0006889Intellectual disability, borderline
HP:0025100Abnormal hippocampus morphology
HP:0032388Periventricular nodular heterotopia
HP:0045084Limb myoclonus

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы