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Omenn syndrome

ORPHA:39041DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (10)

ADA
adenosine deaminase
Disease-causing germline mutation(s) in
OMIM: 608958
RAG1
recombination activating 1
Disease-causing germline mutation(s) in
OMIM: 179615
RAG2
recombination activating 2
Disease-causing germline mutation(s) in
OMIM: 179616
CHD7
chromodomain helicase DNA binding protein 7
Disease-causing germline mutation(s) in
OMIM: 608892
DCLRE1C
DNA cross-link repair 1C
Disease-causing germline mutation(s) in
OMIM: 605988
IL2RG
interleukin 2 receptor subunit gamma
Disease-causing germline mutation(s) in
OMIM: 308380
LIG4
DNA ligase 4
Disease-causing germline mutation(s) in
OMIM: 601837
RMRP
RNA component of mitochondrial RNA processing endoribonuclease
Disease-causing germline mutation(s) in
OMIM: 157660
IL7R
interleukin 7 receptor
Disease-causing germline mutation(s) in
OMIM: 146661
PSMB10
proteasome 20S subunit beta 10
Disease-causing germline mutation(s) in
OMIM: 176847

Фенотипы (28)

Очень частый (80–99%)8
HP:0001019Erythroderma
HP:0001508Failure to thrive
HP:0001596Alopecia
HP:0002028Chronic diarrhea
HP:0002240Hepatomegaly
HP:0002716Lymphadenopathy
HP:0004332Abnormal lymphocyte morphology
HP:0004430Severe combined immunodeficiency
Частый (30–79%)11
HP:0000958Dry skin
HP:0000969Edema
HP:0000989Pruritus
HP:0001072Thickened skin
HP:0001744Splenomegaly
HP:0001880Eosinophilia
HP:0001945Fever
HP:0001974Leukocytosis
HP:0002090Pneumonia
HP:0007549Desquamation of skin soon after birth
HP:0100840Aplasia/Hypoplasia of the eyebrow
Периодический (5–29%)9
HP:0000100Nephrotic syndrome
HP:0000821Hypothyroidism
HP:0000944Abnormal metaphysis morphology
HP:0001831Short toe
HP:0001903Anemia
HP:0002665Lymphoma
HP:0002960Autoimmunity
HP:0100646Thyroiditis
HP:0100806Sepsis

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы