← Назад

Kearns-Sayre syndrome

ORPHA:480DiseaseAutosomal recessive, Mitochondrial inheritance, Not applicableAdolescent, Adult, Childhood, Infancy

Ассоциированные гены (3)

MT-ATP8
mitochondrially encoded ATP synthase membrane subunit 8
Candidate gene tested in
OMIM: 516070
RRM2B
ribonucleotide reductase regulatory TP53 inducible subunit M2B
Disease-causing germline mutation(s) in
OMIM: 604712
MT-TL1
mitochondrially encoded tRNA-Leu (UUA/G) 1
Candidate gene tested in
OMIM: 590050

Фенотипы (30)

Очень частый (80–99%)3
HP:0000580Pigmentary retinopathy
HP:0000590Progressive external ophthalmoplegia
HP:0001709Third degree atrioventricular block
Частый (30–79%)11
HP:0000365Hearing impairment
HP:0000508Ptosis
HP:0000830Anterior hypopituitarism
HP:0001251Ataxia
HP:0001252Hypotonia
HP:0001315Reduced tendon reflexes
HP:0002922Increased CSF protein concentration
HP:0003200Ragged-red muscle fibers
HP:0003202Skeletal muscle atrophy
HP:0003457EMG abnormality
HP:0004622Progressive intervertebral space narrowing
Периодический (5–29%)16
HP:0000467Neck muscle weakness
HP:0000726Dementia
HP:0000819Diabetes mellitus
HP:0000823Delayed puberty
HP:0000829Hypoparathyroidism
HP:0001324Muscle weakness
HP:0001337Tremor
HP:0001638Cardiomyopathy
HP:0001947Renal tubular acidosis
HP:0002015Dysphagia
HP:0002750Delayed skeletal maturation
HP:0003546Exercise intolerance
HP:0004322Short stature
HP:0004374Hemiplegia/hemiparesis
HP:0012622Chronic kidney disease
HP:0100543Cognitive impairment

Эпидемиология (4)

Point prevalence
1-9 / 100 000
Europe
Point prevalence
1-9 / 1 000 000
Finland
Point prevalence
1-9 / 100 000
United Kingdom
Prevalence at birth
1-9 / 1 000 000
Israel

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы