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Familial or sporadic hemiplegic migraine

ORPHA:569DiseaseAutosomal dominantChildhood

Ассоциированные гены (4)

SCN1A
sodium voltage-gated channel alpha subunit 1
Disease-causing germline mutation(s) in
OMIM: 182389
CACNA1A
calcium voltage-gated channel subunit alpha1 A
Disease-causing germline mutation(s) in
OMIM: 601011
ATP1A2
ATPase Na+/K+ transporting subunit alpha 2
Disease-causing germline mutation(s) in
OMIM: 182340
PRRT2
proline rich transmembrane protein 2
Disease-causing germline mutation(s) in
OMIM: 614386

Фенотипы (51)

Очень частый (80–99%)6
HP:0001324Muscle weakness
HP:0002077Migraine with aura
HP:0002167Abnormality of speech or vocalization
HP:0002353EEG abnormality
HP:0011153Focal motor seizure
HP:0011157Focal sensory seizure
Частый (30–79%)23
HP:0032900Focal manual automatism seizure
HP:0032901Focal pedal automatism seizure
HP:0200149CSF lymphocytic pleiocytosis
HP:0000365Hearing impairment
HP:0000575Scotoma
HP:0000651Diplopia
HP:0001260Dysarthria
HP:0001269Hemiparesis
HP:0001289Confusion
HP:0001308Tongue fasciculations
HP:0002172Postural instability
HP:0002181Cerebral edema
HP:0002321Vertigo
HP:0002922Increased CSF protein concentration
HP:0003401Paresthesia
HP:0004305Involuntary movements
HP:0007240Progressive gait ataxia
HP:0010835Dissociated sensory loss
HP:0011172Complex febrile seizure
HP:0011468Facial tics
HP:0012229CSF pleocytosis
HP:0012508Metamorphopsia
HP:0030786Photopsia
Периодический (5–29%)17
HP:0000360Tinnitus
HP:0001259Coma
HP:0001272Cerebellar atrophy
HP:0002301Hemiplegia
HP:0002381Aphasia
HP:0002463Language impairment
HP:0007209Facial paralysis
HP:0007979Gaze-evoked horizontal nystagmus
HP:0008959Distal upper limb muscle weakness
HP:0010544Vertical nystagmus
HP:0010829Impaired temperature sensition
HP:0010833Spontaneous pain sensation
HP:0011199EEG with generalized sharp slow waves
HP:0012044Seesaw nystagmus
HP:0031179Nuchal rigidity
HP:0032044Decreased vigilance
HP:0032506Alien limb phenomenon
Очень редкий (1–4%)5
HP:0001249Intellectual disability
HP:0002133Status epilepticus
HP:0003392First dorsal interossei muscle weakness
HP:0011196EEG with focal sharp waves
HP:0100576Amaurosis fugax

Эпидемиология (2)

Point prevalence
1-5 / 10 000
Europe
Point prevalence
1-5 / 10 000
Denmark

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы