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Autosomal recessive malignant osteopetrosis

ORPHA:667Malformation syndromeAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (4)

CLCN7
chloride voltage-gated channel 7
Disease-causing germline mutation(s) in
OMIM: 602727
TCIRG1
T cell immune regulator 1, ATPase H+ transporting V0 subunit a3
Disease-causing germline mutation(s) (loss of function) in
OMIM: 604592
TNFSF11
TNF superfamily member 11
Disease-causing germline mutation(s) in
OMIM: 602642
SNX10
sorting nexin 10
Disease-causing germline mutation(s) in
OMIM: 614780

Фенотипы (43)

Очень частый (80–99%)35
HP:0000238Hydrocephalus
HP:0000256Macrocephaly
HP:0000365Hearing impairment
HP:0000388Otitis media
HP:0000505Visual impairment
HP:0000639Nystagmus
HP:0000649Abnormality of visual evoked potentials
HP:0000684Delayed eruption of teeth
HP:0000772Abnormal rib morphology
HP:0000774Narrow chest
HP:0000944Abnormal metaphysis morphology
HP:0000980Pallor
HP:0001337Tremor
HP:0001363Craniosynostosis
HP:0001510Growth delay
HP:0001744Splenomegaly
HP:0001903Anemia
HP:0001939Abnormality of metabolism/homeostasis
HP:0002205Recurrent respiratory infections
HP:0002240Hepatomegaly
HP:0002257Chronic rhinitis
HP:0002653Bone pain
HP:0002716Lymphadenopathy
HP:0002757Recurrent fractures
HP:0004349Reduced bone mineral density
HP:0004370Abnormality of temperature regulation
HP:0005930Abnormality of epiphysis morphology
HP:0006323Premature loss of primary teeth
HP:0006487Bowing of the long bones
HP:0007807Optic nerve compression
HP:0008066Abnormal blistering of the skin
HP:0010543Opsoclonus
HP:0010719Abnormality of hair texture
HP:0011002Osteopetrosis
HP:0100022Abnormality of movement
Периодический (5–29%)8
HP:0000978Bruising susceptibility
HP:0001641Abnormal pulmonary valve morphology
HP:0002092Pulmonary arterial hypertension
HP:0002104Apnea
HP:0002148Hypophosphatemia
HP:0002901Hypocalcemia
HP:0004415Pulmonary artery stenosis
HP:0006824Cranial nerve paralysis

Эпидемиология (2)

Prevalence at birth
1-9 / 1 000 000
Europe
Point prevalence
1-9 / 1 000 000
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы