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Amyotrophic lateral sclerosis

ORPHA:803DiseaseAutosomal dominant, Autosomal recessive, Not applicableAdult

Ассоциированные гены (36)

CCNF
cyclin F
Disease-causing germline mutation(s) in
OMIM: 600227
TAF15
TATA-box binding protein associated factor 15
Candidate gene tested in
OMIM: 601574
ANXA11
annexin A11
Disease-causing germline mutation(s) in
OMIM: 602572
CFAP410
cilia and flagella associated protein 410
Disease-causing germline mutation(s) in
OMIM: 603191
GLE1
GLE1 RNA export mediator
Disease-causing germline mutation(s) in
OMIM: 603371
NEK1
NIMA related kinase 1
Major susceptibility factor in
OMIM: 604588
GLT8D1
glycosyltransferase 8 domain containing 1
Major susceptibility factor in
OMIM: 618399
CHCHD10
coiled-coil-helix-coiled-coil-helix domain containing 10
Disease-causing germline mutation(s) in
OMIM: 615903
DAO
D-amino acid oxidase
Disease-causing germline mutation(s) in
OMIM: 124050
ATXN2
ataxin 2
Major susceptibility factor in
OMIM: 601517
CHMP2B
charged multivesicular body protein 2B
Disease-causing germline mutation(s) in
OMIM: 609512
SOD1
superoxide dismutase 1
Disease-causing germline mutation(s) in
OMIM: 147450
TREM2
triggering receptor expressed on myeloid cells 2
Major susceptibility factor in
OMIM: 605086
VAPB
VAMP associated protein B and C
Disease-causing germline mutation(s) in
OMIM: 605704
VCP
valosin containing protein
Disease-causing germline mutation(s) in
OMIM: 601023
NEFH
neurofilament heavy chain
Major susceptibility factor in
OMIM: 162230
OPTN
optineurin
Disease-causing germline mutation(s) in
OMIM: 602432
DCTN1
dynactin subunit 1
Candidate gene tested in
OMIM: 601143
TARDBP
TAR DNA binding protein
Disease-causing germline mutation(s) in
OMIM: 605078
FIG4
FIG4 phosphoinositide 5-phosphatase
Disease-causing germline mutation(s) in
OMIM: 609390
FUS
FUS RNA binding protein
Disease-causing germline mutation(s) in
OMIM: 137070
ANG
angiogenin
Disease-causing germline mutation(s) in
OMIM: 105850
MATR3
matrin 3
Disease-causing germline mutation(s) in
OMIM: 164015
PRPH
peripherin
Major susceptibility factor in
OMIM: 170710
PON1
paraoxonase 1
Disease-causing germline mutation(s) in
OMIM: 168820
PON2
paraoxonase 2
Disease-causing germline mutation(s) in
OMIM: 602447
PON3
paraoxonase 3
Disease-causing germline mutation(s) in
OMIM: 602720
SQSTM1
sequestosome 1
Disease-causing germline mutation(s) in
OMIM: 601530
UBQLN2
ubiquilin 2
Disease-causing germline mutation(s) in
OMIM: 300264
C9ORF72
C9orf72-SMCR8 complex subunit
Disease-causing germline mutation(s) in
OMIM: 614260
PFN1
profilin 1
Disease-causing germline mutation(s) in
OMIM: 176610
TBK1
TANK binding kinase 1
Major susceptibility factor in
OMIM: 604834
HNRNPA1
heterogeneous nuclear ribonucleoprotein A1
Disease-causing germline mutation(s) in
OMIM: 164017
PPARGC1A
PPARG coactivator 1 alpha
Modifying germline mutation in
OMIM: 604517
ERBB4
erb-b2 receptor tyrosine kinase 4
Disease-causing germline mutation(s) in
OMIM: 600543
UNC13A
unc-13 homolog A
Major susceptibility factor in
OMIM: 609894

Фенотипы (47)

Облигатный (100%)1
HP:0007354Amyotrophic lateral sclerosis
Очень частый (80–99%)3
HP:0002180Neurodegeneration
HP:0003324Generalized muscle weakness
HP:0007373Motor neuron atrophy
Частый (30–79%)32
HP:0000217Xerostomia
HP:0000708Atypical behavior
HP:0000712Emotional lability
HP:0000716Depression
HP:0000739Anxiety
HP:0001257Spasticity
HP:0001260Dysarthria
HP:0001347Hyperreflexia
HP:0001618Dysphonia
HP:0001824Weight loss
HP:0002015Dysphagia
HP:0002094Dyspnea
HP:0002307Drooling
HP:0002380Fasciculations
HP:0002878Respiratory failure
HP:0003202Skeletal muscle atrophy
HP:0003394Muscle spasm
HP:0003470Paralysis
HP:0003484Upper limb muscle weakness
HP:0003487Babinski sign
HP:0003693Distal amyotrophy
HP:0007340Lower limb muscle weakness
HP:0008955Progressive distal muscular atrophy
HP:0012378Fatigue
HP:0012473Tongue atrophy
HP:0012531Pain
HP:0030192Fatigable weakness of bulbar muscles
HP:0030195Fatigable weakness of swallowing muscles
HP:0030196Fatigable weakness of respiratory muscles
HP:0030878Abnormality on pulmonary function testing
HP:0031993Hoffmann sign
HP:0100543Cognitive impairment
Периодический (5–29%)10
HP:0001308Tongue fasciculations
HP:0002145Frontotemporal dementia
HP:0002313Spastic paraparesis
HP:0002360Sleep abnormality
HP:0002463Language impairment
HP:0003376Steppage gait
HP:0004326Cachexia
HP:0009027Foot dorsiflexor weakness
HP:0012764Orthopnea
HP:0033683Jaw hyperreflexia
Очень редкий (1–4%)1
HP:0025425Laryngospasm

Эпидемиология (33)

Annual incidence
1-9 / 100 000
Europe
Point prevalence
1-9 / 100 000
Europe
Point prevalence
1-9 / 100 000
Worldwide
Annual incidence
1-9 / 100 000
Worldwide
Annual incidence
1-9 / 100 000
United Kingdom
Point prevalence
1-9 / 100 000
United Kingdom
Annual incidence
1-9 / 100 000
Ireland
Point prevalence
1-9 / 100 000
Ireland
Annual incidence
1-9 / 100 000
Finland
Point prevalence
1-9 / 100 000
Finland
Annual incidence
1-9 / 100 000
Canada
Point prevalence
1-9 / 100 000
Canada
Annual incidence
1-9 / 100 000
United States
Annual incidence
1-9 / 100 000
Uruguay
Point prevalence
1-9 / 100 000
Uruguay
Annual incidence
1-9 / 100 000
Denmark
Point prevalence
1-9 / 100 000
Denmark
Annual incidence
1-9 / 100 000
Italy
Point prevalence
1-9 / 100 000
Italy
Annual incidence
1-9 / 100 000
France
Annual incidence
1-9 / 100 000
Spain
Point prevalence
1-9 / 100 000
Spain
Annual incidence
1-9 / 100 000
Norway
Point prevalence
1-9 / 100 000
Norway
Annual incidence
1-9 / 1 000 000
Taiwan, Province of China
Point prevalence
1-9 / 100 000
Taiwan, Province of China
Annual incidence
1-9 / 100 000
Faroe Islands
Annual incidence
1-9 / 1 000 000
Iran, Islamic Republic of
Point prevalence
1-9 / 100 000
Iran, Islamic Republic of
Annual incidence
1-9 / 100 000
Specific population
Point prevalence
1-5 / 10 000
Specific population
Annual incidence
1-9 / 100 000
Specific population
Point prevalence
1-9 / 100 000
Specific population

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы