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Xeroderma pigmentosum

ORPHA:910DiseaseAutosomal recessiveAll ages

Ассоциированные гены (7)

XPA
XPA, DNA damage recognition and repair factor
Disease-causing germline mutation(s) in
OMIM: 611153
ERCC3
ERCC excision repair 3, TFIIH core complex helicase subunit
Disease-causing germline mutation(s) in
OMIM: 133510
XPC
XPC complex subunit, DNA damage recognition and repair factor
Disease-causing germline mutation(s) in
OMIM: 613208
DDB2
damage specific DNA binding protein 2
Disease-causing germline mutation(s) in
OMIM: 600811
ERCC4
ERCC excision repair 4, endonuclease catalytic subunit
Disease-causing germline mutation(s) in
OMIM: 133520
ERCC5
ERCC excision repair 5, endonuclease
Disease-causing germline mutation(s) in
OMIM: 133530
ERCC2
ERCC excision repair 2, TFIIH core complex helicase subunit
Disease-causing germline mutation(s) in
OMIM: 126340

Фенотипы (59)

Очень частый (80–99%)20
HP:0000135Hypogonadism
HP:0000164Abnormality of the dentition
HP:0000524Conjunctival telangiectasia
HP:0000648Optic atrophy
HP:0000958Dry skin
HP:0000963Thin skin
HP:0000992Cutaneous photosensitivity
HP:0001009Telangiectasia
HP:0001029Poikiloderma
HP:0001072Thickened skin
HP:0001480Freckling
HP:0001508Failure to thrive
HP:0001945Fever
HP:0002353EEG abnormality
HP:0002376Developmental regression
HP:0002829Arthralgia
HP:0006887Intellectual disability, progressive
HP:0012378Fatigue
HP:0100543Cognitive impairment
HP:0100585Telangiectasia of the skin
Частый (30–79%)13
HP:0000028Cryptorchidism
HP:0000407Sensorineural hearing impairment
HP:0000486Strabismus
HP:0000491Keratitis
HP:0000518Cataract
HP:0000962Hyperkeratosis
HP:0001034Hypermelanotic macule
HP:0001053Hypopigmented skin patches
HP:0002861Melanoma
HP:0004334Dermal atrophy
HP:0010783Erythema
HP:0012733Macule
HP:0012740Papilloma
Периодический (5–29%)26
HP:0000252Microcephaly
HP:0000365Hearing impairment
HP:0000498Blepharitis
HP:0000613Photophobia
HP:0000621Entropion
HP:0000656Ectropion
HP:0000995Melanocytic nevus
HP:0001059Pterygium
HP:0001250Seizure
HP:0001251Ataxia
HP:0001257Spasticity
HP:0001315Reduced tendon reflexes
HP:0001596Alopecia
HP:0002071Abnormality of extrapyramidal motor function
HP:0002120Cerebral cortical atrophy
HP:0002664Neoplasm
HP:0002750Delayed skeletal maturation
HP:0003355Aminoaciduria
HP:0004322Short stature
HP:0004493Craniofacial hyperostosis
HP:0007759Opacification of the corneal stroma
HP:0008734Decreased testicular size
HP:0009755Ankyloblepharon
HP:0009830Peripheral neuropathy
HP:0010649Flat nasal alae
HP:0100012Neoplasm of the eye

Эпидемиология (9)

Point prevalence
1-9 / 1 000 000
United States
Point prevalence
1-9 / 100 000
Japan
Prevalence at birth
1-9 / 1 000 000
Europe
Prevalence at birth
1-9 / 1 000 000
United Kingdom
Prevalence at birth
1-9 / 1 000 000
Netherlands
Prevalence at birth
1-9 / 1 000 000
Italy
Prevalence at birth
1-9 / 1 000 000
France
Prevalence at birth
1-9 / 1 000 000
Germany
Annual incidence
1-9 / 100 000
Libyan Arab Jamahiriya

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы