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Full schwannomatosis

ORPHA:93921DiseaseAutosomal dominantAdult, Elderly

Ассоциированные гены (4)

NF2
NF2, moesin-ezrin-radixin like (MERLIN) tumor suppressor
Candidate gene tested in
OMIM: 607379
SMARCB1
SWI/SNF related BAF chromatin remodeling complex subunit B1
Disease-causing germline mutation(s) in
OMIM: 601607
COQ6
coenzyme Q6, monooxygenase
Major susceptibility factor in
OMIM: 614647
LZTR1
leucine zipper like post translational regulator 1
Major susceptibility factor in
OMIM: 600574

Фенотипы (21)

Облигатный (100%)1
HP:0100008Schwannoma
Частый (30–79%)3
HP:0009593Peripheral schwannoma
HP:0010302Spinal cord tumor
HP:0012531Pain
Периодический (5–29%)10
HP:0000131Uterine leiomyoma
HP:0000360Tinnitus
HP:0000365Hearing impairment
HP:0000518Cataract
HP:0001324Muscle weakness
HP:0002650Scoliosis
HP:0002664Neoplasm
HP:0003401Paresthesia
HP:0012032Lipoma
HP:0410275Lumbosacral hemangioma
Очень редкий (1–4%)6
HP:0001250Seizure
HP:0001621Weak voice
HP:0002380Fasciculations
HP:0002858Meningioma
HP:0011750Neoplasm of the anterior pituitary
HP:0033748Hypoesthesia
Исключён (0%)1
HP:0009589Bilateral vestibular schwannoma

Эпидемиология (2)

Point prevalence
Unknown
Worldwide
Annual incidence
<1 / 1 000 000
Finland

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы