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Familial thyroid dyshormonogenesis

ORPHA:95716DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (6)

SLC5A5
solute carrier family 5 member 5
Disease-causing germline mutation(s) in
OMIM: 601843
TPO
thyroid peroxidase
Disease-causing germline mutation(s) in
OMIM: 606765
DUOX2
dual oxidase 2
Disease-causing germline mutation(s) in
OMIM: 606759
DUOXA2
dual oxidase maturation factor 2
Disease-causing germline mutation(s) in
OMIM: 612772
TG
thyroglobulin
Disease-causing germline mutation(s) in
OMIM: 188450
IYD
iodotyrosine deiodinase
Disease-causing germline mutation(s) in
OMIM: 612025

Фенотипы (30)

Очень частый (80–99%)2
HP:0002925Elevated circulating thyroid-stimulating hormone concentration
HP:0031507Decreased circulating thyroxine level
Частый (30–79%)12
HP:0012758Neurodevelopmental delay
HP:0000270Delayed cranial suture closure
HP:0000851Congenital hypothyroidism
HP:0000853Goiter
HP:0001537Umbilical hernia
HP:0002019Constipation
HP:0004491Large posterior fontanelle
HP:0005930Abnormality of epiphysis morphology
HP:0006579Prolonged neonatal jaundice
HP:0008263Thyroid defect in oxidation and organification of iodide
HP:0008828Delayed proximal femoral epiphyseal ossification
HP:0008872Feeding difficulties in infancy
Периодический (5–29%)14
HP:0000158Macroglossia
HP:0000282Facial edema
HP:0001249Intellectual disability
HP:0001252Hypotonia
HP:0001254Lethargy
HP:0001265Hyporeflexia
HP:0001662Bradycardia
HP:0002045Hypothermia
HP:0003265Neonatal hyperbilirubinemia
HP:0005280Depressed nasal bridge
HP:0025482Positive perchlorate discharge test
HP:0025483Abnormal circulating thyroglobulin concentration
HP:0031219Reduced radioactive iodine uptake
HP:0031220Increased radioactive iodine uptake
Очень редкий (1–4%)1
HP:0000407Sensorineural hearing impairment
Исключён (0%)1
HP:0011437Maternal autoimmune disease

Эпидемиология (3)

Annual incidence
1-9 / 100 000
Worldwide
Point prevalence
1-9 / 100 000
Europe
Annual incidence
1-9 / 100 000
Finland

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы