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Rigid spine syndrome

ORPHA:97244DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (2)

ACTA1
actin alpha 1, skeletal muscle
Disease-causing germline mutation(s) in
OMIM: 102610
SELENON
selenoprotein N
Disease-causing germline mutation(s) in
OMIM: 606210

Фенотипы (20)

Очень частый (80–99%)7
HP:0000467Neck muscle weakness
HP:0001290Generalized hypotonia
HP:0002093Respiratory insufficiency
HP:0002650Scoliosis
HP:0003198Myopathy
HP:0003306Spinal rigidity
HP:0011842Abnormality of skeletal morphology
Частый (30–79%)10
HP:0001265Hyporeflexia
HP:0002090Pneumonia
HP:0002421Poor head control
HP:0002987Elbow flexion contracture
HP:0003089Hamstring contractures
HP:0003202Skeletal muscle atrophy
HP:0003273Hip contracture
HP:0003307Hyperlordosis
HP:0030878Abnormality on pulmonary function testing
HP:0031546Cardiac conduction abnormality
Периодический (5–29%)3
HP:0001263Global developmental delay
HP:0002515Waddling gait
HP:0003391Gowers sign

Эпидемиология (3)

Prevalence at birth
Unknown
Worldwide
Point prevalence
Unknown
Worldwide
Point prevalence
1-9 / 1 000 000
United Kingdom

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы