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Sleep-related hypermotor epilepsy

ORPHA:98784DiseaseAutosomal dominantAdolescent, Adult, Childhood

Ассоциированные гены (7)

CHRNA4
cholinergic receptor nicotinic alpha 4 subunit
Disease-causing germline mutation(s) in
OMIM: 118504
CHRNA2
cholinergic receptor nicotinic alpha 2 subunit
Disease-causing germline mutation(s) in
OMIM: 118502
CHRNB2
cholinergic receptor nicotinic beta 2 subunit
Disease-causing germline mutation(s) in
OMIM: 118507
KCNT1
potassium sodium-activated channel subfamily T member 1
Disease-causing germline mutation(s) in
OMIM: 608167
DEPDC5
DEP domain containing 5, GATOR1 subcomplex subunit
Disease-causing germline mutation(s) (loss of function) in
OMIM: 614191
CRH
corticotropin releasing hormone
Disease-causing germline mutation(s) in
OMIM: 122560
CABP4
calcium binding protein 4
Disease-causing germline mutation(s) in
OMIM: 608965

Фенотипы (22)

Очень частый (80–99%)1
HP:0031951Nocturnal seizures
Частый (30–79%)3
HP:0000733Abnormal repetitive mannerisms
HP:0002268Paroxysmal dystonia
HP:0004305Involuntary movements
Периодический (5–29%)12
HP:0000020Urinary incontinence
HP:0000716Depression
HP:0000739Anxiety
HP:0002883Hyperventilation
HP:0011174Hyperkinetic seizures
HP:0011182Interictal epileptiform activity
HP:0011193EEG with focal spikes
HP:0025236Somnambulism
HP:0025237Confusional arousal
HP:0031535Increased theta frequency activity in EEG
HP:0031589Suicidal ideation
HP:0100543Cognitive impairment
Очень редкий (1–4%)6
HP:0000708Atypical behavior
HP:0001256Intellectual disability, mild
HP:0001345Psychotic mentation
HP:0002069Bilateral tonic-clonic seizure
HP:0007018Attention deficit hyperactivity disorder
HP:0025235Non-rapid eye movement parasomnia

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
Unknown
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы