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Behavioral variant of frontotemporal dementia

ORPHA:275864DiseaseAutosomal dominantAdult

Ассоциированные гены (9)

TMEM106B
transmembrane protein 106B
Major susceptibility factor in
OMIM: 613413
PSEN1
presenilin 1
Disease-causing germline mutation(s) in
OMIM: 104311
CHMP2B
charged multivesicular body protein 2B
Major susceptibility factor in
OMIM: 609512
TREM2
triggering receptor expressed on myeloid cells 2
Major susceptibility factor in
OMIM: 605086
VCP
valosin containing protein
Major susceptibility factor in
OMIM: 601023
MAPT
microtubule associated protein tau
Major susceptibility factor in
OMIM: 157140
GRN
granulin precursor
Major susceptibility factor in
OMIM: 138945
SQSTM1
sequestosome 1
Disease-causing germline mutation(s) in
OMIM: 601530
C9ORF72
C9orf72-SMCR8 complex subunit
Major susceptibility factor in
OMIM: 614260

Фенотипы (40)

Очень частый (80–99%)25
HP:0000474Thickened nuchal skin fold
HP:0000708Atypical behavior
HP:0000710Hyperorality
HP:0000711Restlessness
HP:0000718Aggressive behavior
HP:0000719Inappropriate behavior
HP:0000723Restrictive behavior
HP:0000733Abnormal repetitive mannerisms
HP:0000734Disinhibition
HP:0000737Irritability
HP:0000751Personality changes
HP:0000757Lack of insight
HP:0001268Mental deterioration
HP:0002145Frontotemporal dementia
HP:0002354Memory impairment
HP:0002371Loss of speech
HP:0002381Aphasia
HP:0002442Dyscalculia
HP:0002465Poor speech
HP:0006892Frontotemporal cerebral atrophy
HP:0010522Dyslexia
HP:0010526Dysgraphia
HP:0010529Echolalia
HP:0030213Emotional blunting
HP:0030223Perseveration
Частый (30–79%)4
HP:0002500Abnormal cerebral white matter morphology
HP:0011204EEG with continuous slow activity
HP:0012658Abnormal brain FDG positron emission tomography
HP:0030212Collectionism
Периодический (5–29%)11
HP:0000709Psychosis
HP:0000741Apathy
HP:0001288Gait disturbance
HP:0001347Hyperreflexia
HP:0002069Bilateral tonic-clonic seizure
HP:0002071Abnormality of extrapyramidal motor function
HP:0002300Mutism
HP:0002380Fasciculations
HP:0002446Astrocytosis
HP:0002493Upper motor neuron dysfunction
HP:0012671Abulia

Эпидемиология (1)

Point prevalence
1-9 / 100 000
Netherlands

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы