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Microform holoprosencephaly

ORPHA:280200Malformation syndromeMultigenic/multifactorialChildhood, Infancy, Neonatal

Ассоциированные гены (16)

FGFR1
fibroblast growth factor receptor 1
Candidate gene tested in
OMIM: 136350
SUFU
SUFU negative regulator of hedgehog signaling
Candidate gene tested in
OMIM: 607035
PTCH1
patched 1
Disease-causing germline mutation(s) in
OMIM: 601309
SIX3
SIX homeobox 3
Disease-causing germline mutation(s) in
OMIM: 603714
TGIF1
TGFB induced factor homeobox 1
Disease-causing germline mutation(s) in
OMIM: 602630
ZIC2
Zic family zinc finger 2
Disease-causing germline mutation(s) in
OMIM: 603073
GLI2
GLI family zinc finger 2
Disease-causing germline mutation(s) in
OMIM: 165230
CRIPTO
cripto, EGF-CFC family member
Disease-causing germline mutation(s) in
OMIM: 187395
FOXH1
forkhead box H1
Disease-causing germline mutation(s) in
OMIM: 603621
FGF8
fibroblast growth factor 8
Disease-causing germline mutation(s) in
OMIM: 600483
DISP1
dispatched RND transporter family member 1
Disease-causing germline mutation(s) in
OMIM: 607502
CDON
cell adhesion associated, oncogene regulated
Disease-causing germline mutation(s) in
OMIM: 608707
NODAL
nodal growth differentiation factor
Disease-causing germline mutation(s) in
OMIM: 601265
DLL1
delta like canonical Notch ligand 1
Disease-causing germline mutation(s) in
OMIM: 606582
GAS1
growth arrest specific 1
Disease-causing germline mutation(s) in
OMIM: 139185
SHH
sonic hedgehog signaling molecule
Disease-causing germline mutation(s) in
OMIM: 600725

Фенотипы (35)

Очень частый (80–99%)3
HP:0000453Choanal atresia
HP:0006315Single median maxillary incisor
HP:0010644Midnasal stenosis
Частый (30–79%)9
HP:0000252Microcephaly
HP:0000322Short philtrum
HP:0000446Narrow nasal bridge
HP:0000601Hypotelorism
HP:0001249Intellectual disability
HP:0001511Intrauterine growth retardation
HP:0001622Premature birth
HP:0004322Short stature
HP:0010804Tented upper lip vermilion
Периодический (5–29%)23
HP:0000062Ambiguous genitalia
HP:0000104Renal agenesis
HP:0000175Cleft palate
HP:0000202Orofacial cleft
HP:0000463Anteverted nares
HP:0000486Strabismus
HP:0000612Iris coloboma
HP:0000821Hypothyroidism
HP:0000871Panhypopituitarism
HP:0001028Hemangioma
HP:0001250Seizure
HP:0001274Agenesis of corpus callosum
HP:0001360Holoprosencephaly
HP:0001636Tetralogy of Fallot
HP:0002099Asthma
HP:0002247Duodenal atresia
HP:0002650Scoliosis
HP:0003196Short nose
HP:0003458EMG: myopathic abnormalities
HP:0008736Hypoplasia of penis
HP:0009800Maternal diabetes
HP:0009914Cyclopia
HP:0030680Abnormal cardiovascular system morphology

Эпидемиология (1)

Point prevalence
1-9 / 100 000
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы