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Bartter syndrome type 4

ORPHA:89938Clinical subtypeAutosomal recessiveAntenatal

Ассоциированные гены (3)

BSND
barttin CLCNK type accessory subunit beta
Disease-causing germline mutation(s) in
OMIM: 606412
CLCNKB
chloride voltage-gated channel Kb
Disease-causing germline mutation(s) (loss of function) in
OMIM: 602023
CLCNKA
chloride voltage-gated channel Ka
Disease-causing germline mutation(s) (loss of function) in
OMIM: 602024

Фенотипы (36)

Очень частый (80–99%)8
HP:0000127Renal salt wasting
HP:0000841Hyperactive renin-angiotensin system
HP:0000848Increased circulating renin level
HP:0000859Hyperaldosteronism
HP:0001960Hypokalemic metabolic alkalosis
HP:0002900Hypokalemia
HP:0004727Impaired renal concentrating ability
HP:0008619Bilateral sensorineural hearing impairment
Частый (30–79%)16
HP:0001252Hypotonia
HP:0001270Motor delay
HP:0001324Muscle weakness
HP:0001508Failure to thrive
HP:0001518Small for gestational age
HP:0001561Polyhydramnios
HP:0001622Premature birth
HP:0002150Hypercalciuria
HP:0002902Hyponatremia
HP:0002917Hypomagnesemia
HP:0003081Increased urinary potassium
HP:0003113Hypochloremia
HP:0003527Hyperprostaglandinuria
HP:0012622Chronic kidney disease
HP:0025335Delayed ability to stand
HP:0031936Delayed ability to walk
Периодический (5–29%)9
HP:0000121Nephrocalcinosis
HP:0000712Emotional lability
HP:0001525Severe failure to thrive
HP:0001919Acute kidney injury
HP:0001944Dehydration
HP:0002013Vomiting
HP:0002312Clumsiness
HP:0003774Stage 5 chronic kidney disease
HP:0040288Nasogastric tube feeding
Очень редкий (1–4%)2
HP:0000325Triangular face
HP:0000411Protruding ear
Исключён (0%)1
HP:0000822Hypertension

Эпидемиология (1)

Point prevalence
Unknown
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы