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Autosomal dominant cutis laxa

ORPHA:90348DiseaseAutosomal dominantInfancy, Neonatal

Ассоциированные гены (3)

ALDH18A1
aldehyde dehydrogenase 18 family member A1
Disease-causing germline mutation(s) in
OMIM: 138250
FBLN5
fibulin 5
Disease-causing germline mutation(s) in
OMIM: 604580
ELN
elastin
Disease-causing germline mutation(s) in
OMIM: 130160

Фенотипы (59)

Очень частый (80–99%)6
HP:0000973Cutis laxa
HP:0000974Hyperextensible skin
HP:0001582Redundant skin
HP:0007522Increased number of skin folds
HP:0025167Fragmented elastic fibers in the dermis
HP:0100678Premature skin wrinkling
Частый (30–79%)9
HP:0001382Joint hypermobility
HP:0000023Inguinal hernia
HP:0001653Mitral regurgitation
HP:0001659Aortic regurgitation
HP:0001999Abnormal facial shape
HP:0004942Aortic aneurysm
HP:0007495Prematurely aged appearance
HP:0010674Abnormality of the curvature of the vertebral column
HP:0100790Hernia
Периодический (5–29%)34
HP:0000015Bladder diverticulum
HP:0000252Microcephaly
HP:0000270Delayed cranial suture closure
HP:0000325Triangular face
HP:0000337Broad forehead
HP:0000369Low-set ears
HP:0000411Protruding ear
HP:0000486Strabismus
HP:0000508Ptosis
HP:0000519Developmental cataract
HP:0001181Adducted thumb
HP:0001252Hypotonia
HP:0001263Global developmental delay
HP:0001270Motor delay
HP:0001348Brisk reflexes
HP:0001511Intrauterine growth retardation
HP:0001635Congestive heart failure
HP:0001680Coarctation of aorta
HP:0002097Emphysema
HP:0002110Bronchiectasis
HP:0002256Small bowel diverticula
HP:0002650Scoliosis
HP:0002827Hip dislocation
HP:0004969Peripheral pulmonary artery stenosis
HP:0005989Redundant neck skin
HP:0006698Dilatation of the ventricular cavity
HP:0007957Corneal opacity
HP:0008897Postnatal growth retardation
HP:0010648Dermal translucency
HP:0011220Prominent forehead
HP:0011950Bronchiolitis
HP:0011968Feeding difficulties
HP:0012330Pyelonephritis
HP:0100512Low levels of vitamin D
Очень редкий (1–4%)10
HP:0000122Unilateral renal agenesis
HP:0000729Autistic behavior
HP:0000938Osteopenia
HP:0001762Talipes equinovarus
HP:0001763Pes planus
HP:0001884Talipes calcaneovalgus
HP:0002013Vomiting
HP:0002645Wormian bones
HP:0002677Small foramen magnum
HP:0002816Genu recurvatum

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы