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Autosomal recessive primary microcephaly

ORPHA:2512Etiological subtypeAutosomal recessiveAntenatal, Neonatal

Ассоциированные гены (29)

WARS1
tryptophanyl-tRNA synthetase 1
Disease-causing germline mutation(s) in
OMIM: 191050
SARS1
seryl-tRNA synthetase 1
Disease-causing germline mutation(s) in
OMIM: 607529
CIT
citron rho-interacting serine/threonine kinase
Disease-causing germline mutation(s) in
OMIM: 605629
NUP37
nucleoporin 37
Disease-causing germline mutation(s) in
OMIM: 609264
NCAPD3
non-SMC condensin II complex subunit D3
Disease-causing germline mutation(s) in
OMIM: 609276
CENPE
centromere protein E
Disease-causing germline mutation(s) in
OMIM: 117143
COPB2
coat protein complex I subunit beta 2
Disease-causing germline mutation(s) in
OMIM: 606990
PDCD6IP
programmed cell death 6 interacting protein
Disease-causing germline mutation(s) in
OMIM: 608074
TRAPPC10
trafficking protein particle complex subunit 10
Disease-causing germline mutation(s) in
OMIM: 602103
MCM7
minichromosome maintenance complex component 7
Disease-causing germline mutation(s) in
OMIM: 600592
METTL5
methyltransferase 5, N6-adenosine
Disease-causing germline mutation(s) in
OMIM: 618628
TRAPPC14
trafficking protein particle complex subunit 14
Disease-causing germline mutation(s) in
OMIM: 618350
KIF14
kinesin family member 14
Disease-causing germline mutation(s) in
OMIM: 611279
TAF13
TATA-box binding protein associated factor 13
Disease-causing germline mutation(s) in
OMIM: 600774
PYCR2
pyrroline-5-carboxylate reductase 2
Disease-causing germline mutation(s) in
OMIM: 616406
CDK5RAP2
CDK5 regulatory subunit associated protein 2
Disease-causing germline mutation(s) in
OMIM: 608201
CPAP
centrosome assembly and centriole elongation protein
Disease-causing germline mutation(s) in
OMIM: 609279
ASPM
assembly factor for spindle microtubules
Disease-causing germline mutation(s) in
OMIM: 605481
MCPH1
microcephalin 1
Disease-causing germline mutation(s) in
OMIM: 607117
STIL
STIL centriolar assembly protein
Disease-causing germline mutation(s) in
OMIM: 181590
WDR62
WD repeat domain 62
Disease-causing germline mutation(s) in
OMIM: 613583
CEP152
centrosomal protein 152
Disease-causing germline mutation(s) in
OMIM: 613529
CEP135
centrosomal protein 135
Disease-causing germline mutation(s) in
OMIM: 611423
KNL1
kinetochore scaffold 1
Disease-causing germline mutation(s) in
OMIM: 609173
PHC1
polyhomeotic homolog 1
Disease-causing germline mutation(s) in
OMIM: 602978
CDK6
cyclin dependent kinase 6
Disease-causing germline mutation(s) in
OMIM: 603368
SASS6
SAS-6 centriolar assembly protein
Disease-causing germline mutation(s) in
OMIM: 609321
MFSD2A
MFSD2 lysolipid transporter A, lysophospholipid
Disease-causing germline mutation(s) (loss of function) in
OMIM: 614397
ANKLE2
ankyrin repeat and LEM domain containing 2
Disease-causing germline mutation(s) in
OMIM: 616062

Фенотипы (17)

Очень частый (80–99%)9
HP:0000219Thin upper lip vermilion
HP:0000252Microcephaly
HP:0000340Sloping forehead
HP:0000582Upslanted palpebral fissure
HP:0001263Global developmental delay
HP:0001510Growth delay
HP:0002282Gray matter heterotopia
HP:0004322Short stature
HP:0010864Intellectual disability, severe
Частый (30–79%)8
HP:0000076Vesicoureteral reflux
HP:0000122Unilateral renal agenesis
HP:0001274Agenesis of corpus callosum
HP:0001302Pachygyria
HP:0001347Hyperreflexia
HP:0002119Ventriculomegaly
HP:0003103Abnormal cortical bone morphology
HP:0007333Hypoplasia of the frontal lobes

Эпидемиология (3)

Annual incidence
1-9 / 1 000 000
Specific population
Point prevalence
Unknown
Worldwide
Annual incidence
1-9 / 100 000
Pakistan

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы