← Назад

Familial thoracic aortic aneurysm and aortic dissection

ORPHA:91387DiseaseAutosomal dominantAdolescent, Adult, Childhood

Ассоциированные гены (20)

FOXE3
forkhead box E3
Disease-causing germline mutation(s) in
OMIM: 601094
THSD4
thrombospondin type 1 domain containing 4
Disease-causing germline mutation(s) in
OMIM: 614476
SMAD2
SMAD family member 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 601366
LOX
lysyl oxidase
Disease-causing germline mutation(s) (loss of function) in
OMIM: 153455
MAT2A
methionine adenosyltransferase 2A
Candidate gene tested in
OMIM: 601468
ELN
elastin
Candidate gene tested in
OMIM: 130160
HEY2
hes related family bHLH transcription factor with YRPW motif 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 604674
EFEMP2
EGF-like fibulin extracellular matrix protein 2
Disease-causing germline mutation(s) in
OMIM: 604633
TGFB3
transforming growth factor beta 3
Disease-causing germline mutation(s) (loss of function) in
OMIM: 190230
TGFBR1
transforming growth factor beta receptor 1
Disease-causing germline mutation(s) in
OMIM: 190181
TGFBR2
transforming growth factor beta receptor 2
Disease-causing germline mutation(s) in
OMIM: 190182
FBN1
fibrillin 1
Disease-causing germline mutation(s) in
OMIM: 134797
ACTA2
actin alpha 2, smooth muscle
Disease-causing germline mutation(s) in
OMIM: 102620
MYLK
myosin light chain kinase
Disease-causing germline mutation(s) in
OMIM: 600922
SMAD3
SMAD family member 3
Disease-causing germline mutation(s) in
OMIM: 603109
PRKG1
protein kinase cGMP-dependent 1
Disease-causing germline mutation(s) (gain of function) in
OMIM: 176894
MFAP5
microfibril associated protein 5
Disease-causing germline mutation(s) (loss of function) in
OMIM: 601103
TGFB2
transforming growth factor beta 2
Disease-causing germline mutation(s) in
OMIM: 190220
SMAD4
SMAD family member 4
Disease-causing germline mutation(s) in
OMIM: 600993
MYH11
myosin heavy chain 11
Disease-causing germline mutation(s) in
OMIM: 160745

Фенотипы (42)

Очень частый (80–99%)3
HP:0000965Cutis marmorata
HP:0003549Abnormality of connective tissue
HP:0200146Cystic medial necrosis of the aorta
Частый (30–79%)11
HP:0000525Abnormality iris morphology
HP:0000822Hypertension
HP:0001640Cardiomegaly
HP:0001659Aortic regurgitation
HP:0001677Coronaryartery atherosclerosis
HP:0002875Exertional dyspnea
HP:0004933Ascending aortic dissection
HP:0005162Abnormal left ventricular function
HP:0012499Descending aortic dissection
HP:0012763Paroxysmal dyspnea
HP:0100749Chest pain
Периодический (5–29%)28
HP:0012163Carotid artery dilatation
HP:0100775Dural ectasia
HP:0000023Inguinal hernia
HP:0000098Tall stature
HP:0000278Retrognathia
HP:0000316Hypertelorism
HP:0000766Abnormal sternum morphology
HP:0000978Bruising susceptibility
HP:0001166Arachnodactyly
HP:0001297Stroke
HP:0001643Patent ductus arteriosus
HP:0001647Bicuspid aortic valve
HP:0001763Pes planus
HP:0002105Hemoptysis
HP:0002107Pneumothorax
HP:0002138Subarachnoid hemorrhage
HP:0002140Ischemic stroke
HP:0002326Transient ischemic attack
HP:0002616Aortic root aneurysm
HP:0002647Aortic dissection
HP:0002650Scoliosis
HP:0002686Prenatal maternal abnormality
HP:0002705High, narrow palate
HP:0004944Dilatation of the cerebral artery
HP:0004950Peripheral arterial stenosis
HP:0004959Descending thoracic aorta aneurysm
HP:0005112Abdominal aortic aneurysm
HP:0011106Hypovolemia

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы