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Neonatal adrenoleukodystrophy

ORPHA:44DiseaseAutosomal recessiveChildhood, Infancy, Neonatal

Ассоциированные гены (13)

PEX2
peroxisomal biogenesis factor 2
Disease-causing germline mutation(s) in
OMIM: 170993
PEX1
peroxisomal biogenesis factor 1
Disease-causing germline mutation(s) in
OMIM: 602136
PEX10
peroxisomal biogenesis factor 10
Disease-causing germline mutation(s) in
OMIM: 602859
PEX12
peroxisomal biogenesis factor 12
Disease-causing germline mutation(s) in
OMIM: 601758
PEX13
peroxisomal biogenesis factor 13
Disease-causing germline mutation(s) in
OMIM: 601789
PEX14
peroxisomal biogenesis factor 14
Disease-causing germline mutation(s) in
OMIM: 601791
PEX16
peroxisomal biogenesis factor 16
Disease-causing germline mutation(s) in
OMIM: 603360
PEX19
peroxisomal biogenesis factor 19
Disease-causing germline mutation(s) in
OMIM: 600279
PEX26
peroxisomal biogenesis factor 26
Disease-causing germline mutation(s) in
OMIM: 608666
PEX3
peroxisomal biogenesis factor 3
Disease-causing germline mutation(s) in
OMIM: 603164
PEX5
peroxisomal biogenesis factor 5
Disease-causing germline mutation(s) in
OMIM: 600414
PEX6
peroxisomal biogenesis factor 6
Disease-causing germline mutation(s) in
OMIM: 601498
PEX11B
peroxisomal biogenesis factor 11 beta
Disease-causing germline mutation(s) in
OMIM: 603867

Фенотипы (29)

Очень частый (80–99%)21
HP:0000407Sensorineural hearing impairment
HP:0000431Wide nasal bridge
HP:0000174Abnormal palate morphology
HP:0000268Dolichocephaly
HP:0000348High forehead
HP:0000463Anteverted nares
HP:0000486Strabismus
HP:0000639Nystagmus
HP:0000648Optic atrophy
HP:0001250Seizure
HP:0001252Hypotonia
HP:0001347Hyperreflexia
HP:0001392Abnormality of the liver
HP:0001939Abnormality of metabolism/homeostasis
HP:0002353EEG abnormality
HP:0002376Developmental regression
HP:0004322Short stature
HP:0008207Primary adrenal insufficiency
HP:0011344Severe global developmental delay
HP:0100022Abnormality of movement
HP:0000358Posteriorly rotated ears
Частый (30–79%)8
HP:0000256Macrocephaly
HP:0000260Wide anterior fontanel
HP:0000505Visual impairment
HP:0000508Ptosis
HP:0000518Cataract
HP:0002269Abnormality of neuronal migration
HP:0007598Bilateral single transverse palmar creases
HP:0007703Abnormality of retinal pigmentation

Эпидемиология (2)

Prevalence at birth
1-9 / 100 000
Italy
Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы