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Infantile Refsum disease

ORPHA:772DiseaseAutosomal recessiveAll ages

Ассоциированные гены (13)

PEX2
peroxisomal biogenesis factor 2
Disease-causing germline mutation(s) in
OMIM: 170993
PEX1
peroxisomal biogenesis factor 1
Disease-causing germline mutation(s) in
OMIM: 602136
PEX10
peroxisomal biogenesis factor 10
Disease-causing germline mutation(s) in
OMIM: 602859
PEX12
peroxisomal biogenesis factor 12
Disease-causing germline mutation(s) in
OMIM: 601758
PEX13
peroxisomal biogenesis factor 13
Disease-causing germline mutation(s) in
OMIM: 601789
PEX14
peroxisomal biogenesis factor 14
Disease-causing germline mutation(s) in
OMIM: 601791
PEX16
peroxisomal biogenesis factor 16
Disease-causing germline mutation(s) in
OMIM: 603360
PEX19
peroxisomal biogenesis factor 19
Disease-causing germline mutation(s) in
OMIM: 600279
PEX26
peroxisomal biogenesis factor 26
Disease-causing germline mutation(s) in
OMIM: 608666
PEX3
peroxisomal biogenesis factor 3
Disease-causing germline mutation(s) in
OMIM: 603164
PEX5
peroxisomal biogenesis factor 5
Disease-causing germline mutation(s) in
OMIM: 600414
PEX6
peroxisomal biogenesis factor 6
Disease-causing germline mutation(s) in
OMIM: 601498
PEX11B
peroxisomal biogenesis factor 11 beta
Disease-causing germline mutation(s) in
OMIM: 603867

Фенотипы (27)

Очень частый (80–99%)11
HP:0000505Visual impairment
HP:0000510Rod-cone dystrophy
HP:0000662Nyctalopia
HP:0001133Constriction of peripheral visual field
HP:0001263Global developmental delay
HP:0001508Failure to thrive
HP:0002240Hepatomegaly
HP:0003323Progressive muscle weakness
HP:0004322Short stature
HP:0008167Very long chain fatty acid accumulation
HP:0010571Elevated levels of phytanic acid
Частый (30–79%)7
HP:0000365Hearing impairment
HP:0000407Sensorineural hearing impairment
HP:0000639Nystagmus
HP:0000708Atypical behavior
HP:0001251Ataxia
HP:0001252Hypotonia
HP:0001257Spasticity
Периодический (5–29%)9
HP:0000271Abnormality of the face
HP:0000518Cataract
HP:0000648Optic atrophy
HP:0001250Seizure
HP:0001638Cardiomyopathy
HP:0005930Abnormality of epiphysis morphology
HP:0008064Ichthyosis
HP:0010628Facial palsy
HP:0011675Arrhythmia

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы