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Zellweger syndrome

ORPHA:912DiseaseAutosomal recessiveNeonatal

Ассоциированные гены (13)

PEX11B
peroxisomal biogenesis factor 11 beta
Disease-causing germline mutation(s) in
OMIM: 603867
PEX2
peroxisomal biogenesis factor 2
Disease-causing germline mutation(s) in
OMIM: 170993
PEX1
peroxisomal biogenesis factor 1
Disease-causing germline mutation(s) in
OMIM: 602136
PEX10
peroxisomal biogenesis factor 10
Disease-causing germline mutation(s) in
OMIM: 602859
PEX12
peroxisomal biogenesis factor 12
Disease-causing germline mutation(s) in
OMIM: 601758
PEX13
peroxisomal biogenesis factor 13
Disease-causing germline mutation(s) in
OMIM: 601789
PEX14
peroxisomal biogenesis factor 14
Disease-causing germline mutation(s) in
OMIM: 601791
PEX16
peroxisomal biogenesis factor 16
Disease-causing germline mutation(s) in
OMIM: 603360
PEX19
peroxisomal biogenesis factor 19
Disease-causing germline mutation(s) in
OMIM: 600279
PEX26
peroxisomal biogenesis factor 26
Disease-causing germline mutation(s) in
OMIM: 608666
PEX3
peroxisomal biogenesis factor 3
Disease-causing germline mutation(s) in
OMIM: 603164
PEX5
peroxisomal biogenesis factor 5
Disease-causing germline mutation(s) in
OMIM: 600414
PEX6
peroxisomal biogenesis factor 6
Disease-causing germline mutation(s) in
OMIM: 601498

Фенотипы (55)

Очень частый (80–99%)25
HP:0000377Abnormal pinna morphology
HP:0001522Death in infancy
HP:0002093Respiratory insufficiency
HP:0002240Hepatomegaly
HP:0002353EEG abnormality
HP:0002652Skeletal dysplasia
HP:0004322Short stature
HP:0005280Depressed nasal bridge
HP:0006829Severe muscular hypotonia
HP:0007957Corneal opacity
HP:0008167Very long chain fatty acid accumulation
HP:0008872Feeding difficulties in infancy
HP:0010655Epiphyseal stippling
HP:0012368Flat face
HP:0012736Profound global developmental delay
HP:0100543Cognitive impairment
HP:0000260Wide anterior fontanel
HP:0000286Epicanthus
HP:0000348High forehead
HP:0000431Wide nasal bridge
HP:0000582Upslanted palpebral fissure
HP:0000952Jaundice
HP:0001315Reduced tendon reflexes
HP:0001399Hepatic failure
HP:0001508Failure to thrive
Частый (30–79%)23
HP:0000003Multicystic kidney dysplasia
HP:0000028Cryptorchidism
HP:0000047Hypospadias
HP:0000126Hydronephrosis
HP:0000218High palate
HP:0000252Microcephaly
HP:0000256Macrocephaly
HP:0000347Micrognathia
HP:0000407Sensorineural hearing impairment
HP:0000505Visual impairment
HP:0000518Cataract
HP:0000532Chorioretinal abnormality
HP:0000627Posterior embryotoxon
HP:0000639Nystagmus
HP:0000648Optic atrophy
HP:0001250Seizure
HP:0001622Premature birth
HP:0002021Pyloric stenosis
HP:0002024Malabsorption
HP:0002126Polymicrogyria
HP:0005469Flat occiput
HP:0008665Clitoral hypertrophy
HP:0009891Underdeveloped supraorbital ridges
Периодический (5–29%)7
HP:0000157Abnormality of the tongue
HP:0000474Thickened nuchal skin fold
HP:0000501Glaucoma
HP:0001088Brushfield spots
HP:0001629Ventricular septal defect
HP:0001928Abnormality of coagulation
HP:0008207Primary adrenal insufficiency

Эпидемиология (4)

Point prevalence
Unknown
Worldwide
Point prevalence
1-9 / 100 000
Specific population
Prevalence at birth
1-9 / 100 000
Israel
Prevalence at birth
1-9 / 100 000
Specific population

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы