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Non-specific early-onset epileptic encephalopathy

ORPHA:442835DiseaseAutosomal dominant, Autosomal recessive, Not applicable, X-linked recessiveInfancy, Neonatal

Ассоциированные гены (54)

ACTL6B
actin like 6B
Disease-causing germline mutation(s) in
OMIM: 612458
GABRG2
gamma-aminobutyric acid type A receptor subunit gamma2
Disease-causing germline mutation(s) in
OMIM: 137164
GABRA2
gamma-aminobutyric acid type A receptor subunit alpha2
Disease-causing germline mutation(s) in
OMIM: 137140
FZR1
fizzy and cell division cycle 20 related 1
Disease-causing germline mutation(s) in
OMIM: 603619
GABRA5
gamma-aminobutyric acid type A receptor subunit alpha5
Disease-causing germline mutation(s) in
OMIM: 137142
PACS2
phosphofurin acidic cluster sorting protein 2
Disease-causing germline mutation(s) in
OMIM: 610423
YWHAG
tyrosine 3-monooxygenase/tryptophan 5-monooxygenase activation protein gamma
Disease-causing germline mutation(s) in
OMIM: 605356
UBA5
ubiquitin like modifier activating enzyme 5
Disease-causing germline mutation(s) (loss of function) in
OMIM: 610552
GRIN2D
glutamate ionotropic receptor NMDA type subunit 2D
Disease-causing germline mutation(s) (gain of function) in
OMIM: 602717
DALRD3
DALR anticodon binding domain containing 3
Disease-causing germline mutation(s) (loss of function) in
OMIM: 618904
TRAK1
trafficking kinesin protein 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 608112
SLC1A2
solute carrier family 1 member 2
Disease-causing germline mutation(s) in
OMIM: 600300
AP3B2
adaptor related protein complex 3 subunit beta 2
Disease-causing germline mutation(s) in
OMIM: 602166
ATP6V1A
ATPase H+ transporting V1 subunit A
Disease-causing germline mutation(s) in
OMIM: 607027
SCN3A
sodium voltage-gated channel alpha subunit 3
Disease-causing germline mutation(s) in
OMIM: 182391
GABRB2
gamma-aminobutyric acid type A receptor subunit beta2
Disease-causing germline mutation(s) in
OMIM: 600232
CLTC
clathrin heavy chain
Disease-causing germline mutation(s) in
OMIM: 118955
DEPDC5
DEP domain containing 5, GATOR1 subcomplex subunit
Disease-causing germline mutation(s) in
OMIM: 614191
NUS1
NUS1 dehydrodolichyl diphosphate synthase subunit
Disease-causing germline mutation(s) in
OMIM: 610463
CYFIP2
cytoplasmic FMR1 interacting protein 2
Disease-causing germline mutation(s) in
OMIM: 606323
FBXO28
F-box protein 28
Disease-causing germline mutation(s) in
OMIM: 609100
NTRK2
neurotrophic receptor tyrosine kinase 2
Disease-causing germline mutation(s) in
OMIM: 600456
KCNC2
potassium voltage-gated channel subfamily C member 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 176256
KCNH5
potassium voltage-gated channel subfamily H member 5
Disease-causing germline mutation(s) in
OMIM: 605716
SLC38A3
solute carrier family 38 member 3
Disease-causing germline mutation(s) in
OMIM: 604437
FGF12
fibroblast growth factor 12
Disease-causing germline mutation(s) (gain of function) in
OMIM: 601513
SZT2
SZT2 subunit of KICSTOR complex
Disease-causing germline mutation(s) in
OMIM: 615463
CELF2
CUGBP Elav-like family member 2
Disease-causing germline mutation(s) in
OMIM: 602538
DHDDS
dehydrodolichyl diphosphate synthase subunit
Disease-causing germline mutation(s) in
OMIM: 608172
PPP3CA
protein phosphatase 3 catalytic subunit alpha
Disease-causing germline mutation(s) in
OMIM: 114105
SYNJ1
synaptojanin 1
Disease-causing germline mutation(s) in
OMIM: 604297
FOXG1
forkhead box G1
Disease-causing germline mutation(s) in
OMIM: 164874
SYNGAP1
synaptic Ras GTPase activating protein 1
Candidate gene tested in
OMIM: 603384
SCN1A
sodium voltage-gated channel alpha subunit 1
Disease-causing germline mutation(s) in
OMIM: 182389
AARS1
alanyl-tRNA synthetase 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 601065
SCN8A
sodium voltage-gated channel alpha subunit 8
Disease-causing germline mutation(s) (gain of function) in
OMIM: 600702
NECAP1
NECAP endocytosis associated 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 611623
HCN1
hyperpolarization activated cyclic nucleotide gated potassium channel 1
Disease-causing germline mutation(s) (gain of function) in
OMIM: 602780
SLC13A5
solute carrier family 13 member 5
Disease-causing germline mutation(s) in
OMIM: 608305
KCNB1
potassium voltage-gated channel subfamily B member 1
Disease-causing germline mutation(s) in
OMIM: 600397
DNM1
dynamin 1
Disease-causing germline mutation(s) in
OMIM: 602377
KCNA2
potassium voltage-gated channel subfamily A member 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 176262
KCNA2
potassium voltage-gated channel subfamily A member 2
Disease-causing germline mutation(s) (gain of function) in
OMIM: 176262
EEF1A2
eukaryotic translation elongation factor 1 alpha 2
Disease-causing germline mutation(s) in
OMIM: 602959
CNKSR2
connector enhancer of kinase suppressor of Ras 2
Disease-causing germline mutation(s) in
OMIM: 300724
PARS2
prolyl-tRNA synthetase 2, mitochondrial
Disease-causing germline mutation(s) in
OMIM: 612036
UFSP2
UFM1 specific peptidase 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 611482
ATP1A2
ATPase Na+/K+ transporting subunit alpha 2
Disease-causing germline mutation(s) in
OMIM: 182340
ATP1A3
ATPase Na+/K+ transporting subunit alpha 3
Disease-causing germline mutation(s) in
OMIM: 182350
GABBR2
gamma-aminobutyric acid type B receptor subunit 2
Disease-causing germline mutation(s) in
OMIM: 607340
CACNA1B
calcium voltage-gated channel subunit alpha1 B
Disease-causing germline mutation(s) (loss of function) in
OMIM: 601012
CDK19
cyclin dependent kinase 19
Disease-causing germline mutation(s) in
OMIM: 614720
CACNA1A
calcium voltage-gated channel subunit alpha1 A
Disease-causing germline mutation(s) in
OMIM: 601011
CACNA2D1
calcium voltage-gated channel auxiliary subunit alpha2delta 1
Disease-causing germline mutation(s) in
OMIM: 114204

Фенотипы (48)

Очень частый (80–99%)1
HP:0001298Encephalopathy
Частый (30–79%)10
HP:0000750Delayed speech and language development
HP:0001249Intellectual disability
HP:0001250Seizure
HP:0001263Global developmental delay
HP:0001265Hyporeflexia
HP:0001290Generalized hypotonia
HP:0001508Failure to thrive
HP:0002376Developmental regression
HP:0010844EEG with multifocal slow activity
HP:0011443Abnormality of coordination
Периодический (5–29%)31
HP:0000252Microcephaly
HP:0000348High forehead
HP:0000494Downslanted palpebral fissures
HP:0000508Ptosis
HP:0000639Nystagmus
HP:0000668Hypodontia
HP:0000708Atypical behavior
HP:0000717Autism
HP:0001251Ataxia
HP:0001257Spasticity
HP:0001268Mental deterioration
HP:0001273Abnormal corpus callosum morphology
HP:0001288Gait disturbance
HP:0001315Reduced tendon reflexes
HP:0001336Myoclonus
HP:0001337Tremor
HP:0001558Decreased fetal movement
HP:0002020Gastroesophageal reflux
HP:0002059Cerebral atrophy
HP:0002063Rigidity
HP:0002317Unsteady gait
HP:0002421Poor head control
HP:0002521Hypsarrhythmia
HP:0004305Involuntary movements
HP:0004322Short stature
HP:0007018Attention deficit hyperactivity disorder
HP:0011968Feeding difficulties
HP:0012444Brain atrophy
HP:0012447Abnormal myelination
HP:0100660Dyskinesia
HP:0100710Impulsivity
Очень редкий (1–4%)6
HP:0000504Abnormality of vision
HP:0000546Retinal degeneration
HP:0000648Optic atrophy
HP:0002133Status epilepticus
HP:0002509Limb hypertonia
HP:0012547Abnormal involuntary eye movements

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы